van Grotel M, Meijerink J P P, van Wering E R, Langerak A W, Beverloo H B, Buijs-Gladdines J G C A M, Burger N B, Passier M, van Lieshout E M, Kamps W A, Veerman A J P, van Noesel M M, Pieters R
Department of Pediatric Oncology/Hematology, Erasmus University Medical Center-Sophia Children's Hospital, Rotterdam, The Netherlands.
Leukemia. 2008 Jan;22(1):124-31. doi: 10.1038/sj.leu.2404957. Epub 2007 Oct 11.
Pediatric T-cell acute lymphoblastic leukemia (T-ALL) is characterized by chromosomal rearrangements possibly enforcing arrest at specific development stages. We studied the relationship between molecular-cytogenetic abnormalities and T-cell development stage to investigate whether arrest at specific stages can explain the prognostic significance of specific abnormalities. We extensively studied 72 pediatric T-ALL cases for genetic abnormalities and expression of transcription factors, NOTCH1 mutations and expression of specific CD markers. HOX11 cases were CD1 positive consistent with a cortical stage, but as 4/5 cases lacked cytoplasmatic-beta expression, developmental arrest may precede beta-selection. HOX11L2 was especially confined to immature and pre-AB developmental stages, but 3/17 HOX11L2 mature cases were restricted to the gammadelta-lineage. TAL1 rearrangements were restricted to the alphabeta-lineage with most cases being TCR-alphabeta positive. NOTCH1 mutations were present in all molecular-cytogenetic subgroups without restriction to a specific developmental stage. CALM-AF10 was associated with early relapse. TAL1 or HOX11L2 rearrangements were associated with trends to good and poor outcomes, respectively. Also cases with high vs low TAL1 expression levels demonstrated a trend toward good outcome. Most cases with lower TAL1 levels were HOX11L2 or CALM-AF10 positive. NOTCH1 mutations did not predict for outcome. Classification into T-cell developmental subgroups was not predictive for outcome.
小儿T细胞急性淋巴细胞白血病(T-ALL)的特征是可能在特定发育阶段发生染色体重排,从而导致细胞停滞。我们研究了分子细胞遗传学异常与T细胞发育阶段之间的关系,以探讨特定阶段的停滞是否可以解释特定异常的预后意义。我们广泛研究了72例小儿T-ALL病例的基因异常、转录因子表达、NOTCH1突变以及特定CD标志物的表达。HOX11病例CD1呈阳性,与皮质阶段一致,但由于4/5的病例缺乏细胞质β表达,发育停滞可能先于β选择。HOX11L2特别局限于未成熟和前AB发育阶段,但17例HOX11L2成熟病例中有3例仅限于γδ谱系。TAL1重排仅限于αβ谱系,大多数病例TCR-αβ呈阳性。NOTCH1突变存在于所有分子细胞遗传学亚组中,不受特定发育阶段的限制。CALM-AF10与早期复发相关。TAL1或HOX11L2重排分别与良好和不良预后的趋势相关。TAL1表达水平高与低的病例也显示出良好预后的趋势。大多数TAL1水平较低的病例HOX11L2或CALM-AF10呈阳性。NOTCH1突变不能预测预后。分类为T细胞发育亚组对预后没有预测作用。