Aslan S, Yavuz H, Cagici A C, Kizilkilic O
Department of Otorhinolaryngology, Baskent University, Ankara, Turkey.
J Laryngol Otol. 2008 Jul;122(7):737-40. doi: 10.1017/S0022215108001977. Epub 2008 Mar 11.
To report the case of a spontaneous arteriovenous malformation involving the auricula, external auditory meatus, middle ear and part of the petrous apex, and also to provide updated information about its management.
A 33-year-old woman presented complaining of accelerated growth of a retro-auricular swelling during her latest pregnancy, together with pain, pulsatile tinnitus and ear discharge. An arteriovenous malformation occupying the right auricula, external auditory canal, mastoid process of the temporal bone and the lateral half of the petrous segment was diagnosed, using temporal computerised tomography and magnetic resonance imaging. The lesion was embolised with polyvinyl alcohol particles at angiography. Excision of the arteriovenous malformation nidus was performed. Three years post-operatively, magnetic resonance imaging showed no residual lesion or recurrence at the temporal bone and petrous apex, although a few scanty, serpiginous, vascular remnants had persisted.
In the head and neck, arteriovenous malformations usually occur intracranially; they are rare outside the cranium. To our knowledge, there have been no previously published cases of such an extensive arteriovenous malformation involving the temporal region. Apropos of our case, the definition, clinical findings, diagnostic approaches and therapeutic management of arteriovenous malformations are discussed.
报告一例累及耳廓、外耳道、中耳及部分岩尖的自发性动静脉畸形病例,并提供其治疗的最新信息。
一名33岁女性患者,主诉在其最近一次怀孕期间耳后肿胀加速生长,伴有疼痛、搏动性耳鸣和耳漏。通过颞部计算机断层扫描和磁共振成像,诊断出一个动静脉畸形,占据右耳廓、外耳道、颞骨乳突及岩段外侧半。在血管造影时用聚乙烯醇颗粒对病变进行了栓塞。对动静脉畸形病灶进行了切除。术后三年,磁共振成像显示颞骨和岩尖无残留病灶或复发,尽管仍有一些稀疏、蜿蜒的血管残余。
在头颈部,动静脉畸形通常发生在颅内;颅外罕见。据我们所知,此前尚无关于累及颞区如此广泛的动静脉畸形病例的报道。结合我们的病例,讨论了动静脉畸形的定义、临床表现、诊断方法和治疗管理。