Björklund Peyman, Lindberg Daniel, Akerström Göran, Westin Gunnar
Department of Surgical Sciences, Endocrine Unit, Uppsala University, Uppsala University Hospital, SE-751 85 Uppsala, Sweden.
Mol Cancer. 2008 Jun 9;7:53. doi: 10.1186/1476-4598-7-53.
Aberrant accumulation of beta-catenin plays an important role in a variety of human neoplasms. We recently reported accumulation of beta-catenin in parathyroid adenomas from patients with primary hyperparathyroidism (pHPT). In CTNNB1 exon 3, we detected a stabilizing mutation (S37A) in 3 out of 20 analyzed adenomas. The aim of the present study was to determine the frequency and zygosity of mutations in CTNNB1 exon 3, and beta-catenin accumulation in a large series of parathyroid adenomas of Swedish patients.
The mutation S37A (TCT > GCT) was detected by direct DNA sequencing of PCR fragments in 6 out of 104 sporadic parathyroid adenomas (5.8%). Taking our previous study into account, a total of 9 out of 124 (7.3%) adenomas displayed the same mutation. The mutations were homozygous by DNA sequencing, restriction enzyme cleavage, and gene copy number determination using the GeneChip 500 K Mapping Array Set. All tumors analyzed by immunohistochemistry, including those with mutation, displayed aberrant beta-catenin accumulation. Western blotting revealed a slightly higher expression level of beta-catenin and nonphosphorylated active beta-catenin in tumors with mutation compared to those without. Presence of the mutation was not related to distinct clinical characteristics.
Aberrant accumulation of beta-catenin is very common in parathyroid tumors, and is caused by stabilizing homozygous mutation in 7.3% of Swedish pHPT patients.
β-连环蛋白的异常积聚在多种人类肿瘤中起重要作用。我们最近报道了原发性甲状旁腺功能亢进症(pHPT)患者甲状旁腺腺瘤中β-连环蛋白的积聚情况。在CTNNB1外显子3中,我们在20个分析的腺瘤中有3个检测到一个稳定突变(S37A)。本研究的目的是确定瑞典患者一大系列甲状旁腺腺瘤中CTNNB1外显子3突变的频率和纯合性,以及β-连环蛋白的积聚情况。
通过对PCR片段进行直接DNA测序,在104个散发性甲状旁腺腺瘤中有6个(5.8%)检测到S37A(TCT > GCT)突变。将我们之前的研究考虑在内,124个腺瘤中有9个(7.3%)显示相同的突变。通过DNA测序、限制性内切酶切割以及使用基因芯片500K Mapping Array Set进行基因拷贝数测定,发现这些突变是纯合的。所有通过免疫组织化学分析的肿瘤,包括那些有突变的肿瘤,均显示β-连环蛋白异常积聚。蛋白质印迹分析显示,与无突变的肿瘤相比,有突变的肿瘤中β-连环蛋白和非磷酸化活性β-连环蛋白的表达水平略高。突变的存在与明显的临床特征无关。
β-连环蛋白的异常积聚在甲状旁腺肿瘤中非常常见,在7.3%的瑞典pHPT患者中是由稳定的纯合突变引起的。