Morava E, Wosik H N, Sykut-Cegielska J, Adamowicz M, Guillard M, Wevers R A, Lefeber D J, Cruysberg J R M
Radboud University Nijmegen Medical Centre, Department of Pediatrics, PO Box 9101, 6500 HB Nijmegen, The Netherlands.
Br J Ophthalmol. 2009 Mar;93(3):350-4. doi: 10.1136/bjo.2008.145359. Epub 2008 Nov 19.
Children with congenital disorders of glycosylation (CDG) type Ia frequently present with ocular involvement and visual loss. Little is known, however, about the occurrence of ophthalmological abnormalities in other subtypes of CDG syndrome.
We evaluated 45 children sequentially diagnosed with CDG type I for the presence of ocular abnormalities at the time of the diagnosis and during follow-up. We compared the various ophthalmic findings in the different CDG subgroups.
Of the 45 patients, 22 had CDG type Ia, nine had CDG type Ic and 14 had a so-far undiagnosed biochemical background (CDG type Ix). We found ocular anomalies in 28 of the 45 children. Three had unique findings, including congenital cataract, retinal coloboma and glaucoma. A few CDG type Ia patients showed a sequential occurrence of symptoms, including retinitis pigmentosa or cataract.
Ophthalmic findings are frequent in CDG syndrome involving both the anterior and posterior segment of the eye. The disorder might lead to abnormal development of the lens or the retina, cause diminished vision, alter ocular motility and intraocular pressure. We suggest routine screening and follow-up for ophthalmological anomalies in all children diagnosed with CDG syndrome to provide early treatment and adequate counselling.
I型先天性糖基化障碍(CDG)患儿常伴有眼部受累及视力丧失。然而,对于CDG综合征其他亚型中眼科异常的发生情况知之甚少。
我们对45例先后被诊断为I型CDG的患儿在诊断时及随访期间进行了眼部异常情况评估。我们比较了不同CDG亚组的各种眼科检查结果。
45例患者中,22例为Ia型CDG,9例为Ic型CDG,14例生化背景尚未明确(Ix型CDG)。我们在45例患儿中的28例发现了眼部异常。3例有独特表现,包括先天性白内障、视网膜缺损和青光眼。少数Ia型CDG患者出现了一系列症状,包括色素性视网膜炎或白内障。
在累及眼球前段和后段的CDG综合征中,眼科检查结果很常见。该疾病可能导致晶状体或视网膜发育异常,导致视力下降,影响眼球运动和眼压。我们建议对所有诊断为CDG综合征的患儿进行眼科异常的常规筛查和随访,以便提供早期治疗和适当的咨询。