Cajaiba Mariana M, Reyes-Múgica Miguel
Program of Pediatric and Developmental Pathology, Yale University School of Medicine, New Haven, CT 06520, USA.
Hum Pathol. 2009 Apr;40(4):594-8. doi: 10.1016/j.humpath.2008.09.003. Epub 2008 Dec 11.
We present here an unusual case in which 3 distinct, apparently unrelated clinical entities were diagnosed in a pediatric patient. A 6-year-old female, previously diagnosed with neurofibromatosis type 1, presented with a mediastinal T-cell lymphoblastic lymphoma; the metabolic and molecular confirmation of Gaucher disease were obtained after typical Gaucher cells were found in the patient's bone marrow after a staging biopsy. The morphological and ultrastructural findings leading to the incidental diagnosis of this rare metabolic disorder are illustrated. In addition, we discuss the possible pathogenetic relationships among these 3 distinct clinical entities, as well as the challenges in the differential diagnosis of bone marrow histiocytic infiltrations in patients with hematologic malignancies.
我们在此呈现一个不寻常的病例,一名儿科患者被诊断出患有3种不同的、看似不相关的临床病症。一名6岁女性,此前被诊断为1型神经纤维瘤病,现又患上纵隔T细胞淋巴母细胞淋巴瘤;在分期活检后,患者骨髓中发现典型的戈谢细胞,随后获得了戈谢病的代谢和分子确诊依据。文中展示了导致这一罕见代谢紊乱症被偶然诊断出的形态学和超微结构检查结果。此外,我们还讨论了这3种不同临床病症之间可能的发病机制关系,以及血液系统恶性肿瘤患者骨髓组织细胞浸润鉴别诊断中的挑战。