Ospedale San Luca IRCCS, Istituto Auxologico Italiano, University of Milan, Via Spagnoletto 3, 20149, Milan, Italy.
Pituitary. 2009;12(4):294-6. doi: 10.1007/s11102-009-0174-2.
Differential diagnosis of ACTH-dependent Cushing's syndrome often presents major difficulties. Diagnostic troubles are increased by suboptimal specificity of endocrine tests, the rarity of ectopic ACTH secretion and the frequent incidental discovery of pituitary adenomas. A 43-year-old female reported with mild signs and symptoms of hypercortisolism, and initial hormonal tests and results of pituitary imaging (7-mm adenoma) were suggestive for Cushing's disease. However, inadequate response to corticotrophin-releasing hormone and failure to suppress after 8 mg dexamethasone pointed towards an ectopic source. Total body CT scan visualized only a small, non-specific nodule in the right posterior costophrenic excavation. Inferior petrosal sinus sampling revealed an absent center:periphery ACTH gradient but octreoscan and (18)F-FDG-PET-CT failed to detect abnormal tracer accumulation. We weighed results of the laboratory with those of imaging and decided to remove the lung nodule. Pathology identified a typical, ACTH-staining carcinoid and the diagnosis was confirmed by postsurgical hypoadrenalism. In conclusion, imaging may prove unsatisfactory or even misleading for the etiologial diagnosis of ACTH-dependent Cushing's syndrome and should therefore be interpreted only in context with results of hormonal dynamic testing.
ACTH 依赖性库欣综合征的鉴别诊断常带来重大困难。内分泌测试的特异性不佳、异位 ACTH 分泌的罕见性以及垂体腺瘤的偶然发现增加了诊断上的困难。一名 43 岁女性以轻度库欣综合征体征和症状就诊,初始激素测试和垂体影像学(7mm 腺瘤)结果提示库欣病。然而,促肾上腺皮质激素释放激素刺激试验反应不足,8mg 地塞米松抑制试验后未被抑制,提示为异位来源。全身 CT 扫描仅在右后肋膈角处发现一个小的、非特异性结节。岩下窦取样显示无中心:周围 ACTH 梯度,但奥曲肽扫描和(18)F-FDG-PET-CT 未能检测到异常示踪剂积聚。我们将实验室结果与影像学结果进行权衡,决定切除肺部结节。病理发现了典型的 ACTH 染色类癌,术后肾上腺功能减退证实了这一诊断。总之,影像学对于 ACTH 依赖性库欣综合征的病因诊断可能不理想,甚至具有误导性,因此应仅结合激素动态测试结果进行解读。