Barnard J A, Manci E
Department of Pediatrics, Vanderbilt University Medical Center, Nashville, Tennessee.
Gastroenterology. 1991 Nov;101(5):1420-7. doi: 10.1016/0016-5085(91)90097-5.
A 21-day-old infant presented with anemia, conjugated hyperbilirubinemia, hypoproteinemia, and a severe coagulopathy. The hospital course was marked by progressive hepatic failure, encephalopathy, and renal insufficiency. The infant died on day 15 of hospitalization. Postmortem examination showed diffuse hepatic fibrosis and marked siderosis of the liver, pancreas, kidney, adrenal glands, and the duodenal epithelium, with sparing of the reticuloendothelial system. These findings were characteristic of idiopathic neonatal iron-storage disease. Previously reported cases are summarized and discussed. An increased awareness and understanding of this rapidly fatal disorder will be important for genetic counseling and possibly in defining an aberrant mechanism in the handling of iron.
一名21日龄婴儿出现贫血、结合胆红素血症、低蛋白血症和严重凝血病。住院过程中出现进行性肝衰竭、脑病和肾功能不全。婴儿于住院第15天死亡。尸检显示弥漫性肝纤维化以及肝脏、胰腺、肾脏、肾上腺和十二指肠上皮显著的含铁血黄素沉着,网状内皮系统未受累。这些发现是特发性新生儿铁储存病的特征。对先前报道的病例进行了总结和讨论。提高对这种快速致命疾病的认识和理解对于遗传咨询以及可能确定铁代谢异常机制具有重要意义。