Su Yu-xiong, Liao Gui-qing, Wang Lin, Liang Yu-jie, Chu Mei, Zheng Guang-sen
Department of Oral and Maxillofacial Surgery, Guanghua School of Stomatology, Sun Yat-sen University, Guangzhou, China.
Laryngoscope. 2009 Jul;119(7):1344-7. doi: 10.1002/lary.20514.
OBJECTIVES/HYPOTHESIS: Salivary gland obstruction caused by vascular malformation with phleboliths is relatively uncommon and may be masquerading as sialolithiasis. This article presents the case of a patient who suffered from vascular malformation with phleboliths that caused submandibular gland obstruction and was once misdiagnosed as sialolithiasis.
Illustrative case report and review of the literature.
Our patient was presented with recurrent episodes of right submandibular swelling and pain at mealtime for two years. The radiopacities in the X-ray film were misdiagnosed as multiple sialoliths. The sialendoscopic surgery ruled out the sialoliths, and an impressively expanded vascular network consisting of capillaries was detected all over the ductal lumen. We diagnosed vascular malformation with phleboliths. A search of the MEDLINE database (from 1948 to February 2009) was performed.
The patient was treated with sclerotherapy. The clinical outcome was satisfactory during a follow-up of 28 months, with no evidence of recurrence. The results of the extensive literature review showed that vascular malformation with phleboliths that leads to submandibular gland obstruction is rare with a total of three cases reported, including this patient.
Vascular malformation with phleboliths must be included in the differential diagnosis of salivary gland obstruction.
目的/假设：由伴有静脉石的血管畸形引起的唾液腺梗阻相对少见，可能会被误诊为涎石病。本文介绍了一例患有伴有静脉石的血管畸形导致下颌下腺梗阻且曾被误诊为涎石病的患者病例。
病例报告及文献综述。
我们的患者两年来在进餐时反复出现右侧下颌下肿胀和疼痛。X线片中的不透光区被误诊为多个涎石。涎腺内镜手术排除了涎石，并在整个导管腔内检测到由毛细血管组成的显著扩张的血管网络。我们诊断为伴有静脉石的血管畸形。检索了MEDLINE数据库（1948年至2009年2月）。
患者接受了硬化治疗。在28个月的随访期间临床结果令人满意，无复发迹象。广泛的文献综述结果显示，导致下颌下腺梗阻的伴有静脉石的血管畸形很罕见，包括该患者在内共报告了3例。
伴有静脉石的血管畸形必须纳入唾液腺梗阻的鉴别诊断。
