De Zoysa N, Vasani S, Kaniyur S, Frosh A
Department of Otolaryngology, Lister Hospital, Stevenage, UK.
J Laryngol Otol. 2009 Dec;123(12):1371-4. doi: 10.1017/S0022215109005726. Epub 2009 Jun 23.
We present an extremely rare case of a 44-year-old woman with right gustatory otorrhoea and otalgia.
The patient had been initially treated for otitis externa after Pseudomonas aeruginosa was grown from a microbiological swab. The otorrhoea fluid was collected and tested positive for amylase. Sialography and computed tomography imaging of the temporal bone confirmed a sialo-aural fistula from the right parotid gland to the bony external acoustic meatus. The defect was consistent with a patent foramen of Huschke. The fistula was identified surgically via a superficial parotidectomy approach, after contrast injection of Bonney's blue dye into the parotid duct, and then ligated and divided. The patient had immediate and sustained resolution of her otorrhoea.
Sialo-aural fistulae are extremely rare, and usually arise as a complication of surgery or as an acquired disease process. To date, only four cases have been reported. This case demonstrates the use of sensitive investigation involving sialography and computed tomography, as well as successful surgical management, with complete resolution of symptoms.
我们报告一例极为罕见的44岁女性病例,该患者患有右侧味觉性耳漏和耳痛。
患者最初因外耳道拭子培养出铜绿假单胞菌而被诊断为外耳道炎。收集耳漏液并检测淀粉酶呈阳性。颞骨涎管造影和计算机断层扫描成像证实存在从右侧腮腺到骨性外耳道的涎腺-耳瘘。该缺损与胡施克孔未闭一致。在向腮腺导管内注入邦尼蓝染料造影后,通过浅叶腮腺切除术手术识别出瘘管,然后进行结扎和切断。患者耳漏立即且持续缓解。
涎腺-耳瘘极为罕见,通常作为手术并发症或后天性疾病过程出现。迄今为止,仅报告了4例。本病例展示了使用涎管造影和计算机断层扫描等敏感检查方法,以及成功的手术治疗,症状完全缓解。