Lynch H T, Watson P, Bewtra C, Conway T A, Hippee C R, Kaur P, Lynch J F, Ponder B A
Department of Preventive Medicine/Public Health, Creighton University School of Medicine, Omaha, Nebraska 68178.
Cancer. 1991 Mar 1;67(5):1460-6. doi: 10.1002/1097-0142(19910301)67:5<1460::aid-cncr2820670534>3.0.co;2-s.
An unknown fraction of the ovarian cancer burden occurs in women with a family history indicative of a putative autosomal dominantly inherited cancer susceptibility syndrome. The results from a five-generation, extended, hereditary breast-ovarian cancer kindred are described 10 years after it was initially ascertained. Significantly more cancers were observed in high-risk family members during this decade than were expected (P less than 0.001). The age of ovarian cancer diagnosis was studied in additional ovarian cancer-prone families of three types: site-specific ovarian cancer syndrome, the breast-ovarian cancer syndrome, and Lynch syndrome II. The age of onset in each of the three sets was significantly (P less than 0.001) earlier than the general population mean of 59, and there were significant differences in the age of onset (P = 0.050) among these three cohorts. Ovarian cancer histology was similar to that of patients with negative family histories. There may be clinically significant heterogeneity in the age at diagnosis of ovarian cancer among these ovarian cancer-prone syndromes. This has important implications for understanding its natural history and targeting surveillance-management strategies.
卵巢癌负担中有一部分病因不明,发生在有家族病史的女性中,这些家族病史提示可能存在常染色体显性遗传的癌症易感性综合征。本文描述了一个五代的、扩展的遗传性乳腺癌-卵巢癌家族系谱,该系谱在最初确定后的10年的研究结果。在这十年中,高危家族成员中观察到的癌症显著多于预期(P<0.001)。对另外三种类型的易患卵巢癌家族进行了研究,以了解卵巢癌的诊断年龄:特定部位卵巢癌综合征、乳腺癌-卵巢癌综合征和林奇综合征II型。这三组人群中卵巢癌的发病年龄均显著早于一般人群的平均发病年龄59岁(P<0.001),且这三组人群的发病年龄存在显著差异(P=0.050)。卵巢癌的组织学与家族史阴性的患者相似。在这些易患卵巢癌的综合征中,卵巢癌的诊断年龄可能存在临床上显著的异质性。这对于理解其自然病史以及制定针对性的监测管理策略具有重要意义。