Department of Biotechnology, Hoseo University, 165 Baebang-Myun, Asan, Chungnam, Republic of Korea.
Biochem Biophys Res Commun. 2010 Jan 1;391(1):974-8. doi: 10.1016/j.bbrc.2009.11.177. Epub 2009 Dec 4.
Familial hypokalemic periodic paralysis is an autosomal-dominant channelopathy that features episodic attacks of flaccid paralysis with concomitant hypokalemia. Reduced activity of ATP-sensitive K(+) (K(ATP)) channels is suggested to be responsible for this disorder; however, the molecular mechanisms have not yet been elucidated. In this study, we investigated the molecular mechanism of reduced K(ATP) channel activity in skeletal muscle cells of patients with familial hypokalemic periodic paralysis. We examined the mRNA and protein levels of SUR2A, a K(ATP) channel subunit, in cells from patients (patient cells) and normal individuals (normal cells). Our results demonstrated that normal cells exposed to 50mM potassium buffer, which was used to induce depolarization, did not show significant change in the SUR2A mRNA levels; however, the protein level significantly increased in the cytosolic fraction. When the patient cells were exposed to 50mM potassium buffer, the SUR2A mRNA level significantly decreased. Further, the protein level of SUR2A significantly increased in the membrane fraction but decreased in the cytosolic fraction in patient cells. These findings suggest that abnormal localization of the SUR2A K(+) channel protein leads to reduced K(ATP) channel activity in familial hypokalemic periodic paralysis.
家族性低钾周期性麻痹是一种常染色体显性遗传性离子通道病,其特征为反复发作的弛缓性瘫痪伴低钾血症。提示 ATP 敏感性钾(K(ATP))通道活性降低是导致这种疾病的原因;然而,其分子机制尚未阐明。在这项研究中,我们研究了家族性低钾周期性麻痹患者骨骼肌细胞中 K(ATP)通道活性降低的分子机制。我们检测了患者(患者细胞)和正常个体(正常细胞)中 SUR2A,一种 K(ATP)通道亚基的 mRNA 和蛋白水平。我们的结果表明,暴露于 50mM 钾缓冲液(用于诱导去极化)的正常细胞中 SUR2A mRNA 水平没有明显变化;然而,细胞质部分的蛋白水平显著增加。当患者细胞暴露于 50mM 钾缓冲液时,SUR2A mRNA 水平显著降低。此外,患者细胞中 SUR2A 的蛋白水平在膜部分显著增加,但在细胞质部分减少。这些发现表明,SUR2A K(+)通道蛋白的异常定位导致家族性低钾周期性麻痹中 K(ATP)通道活性降低。