Plesmanlaan 121, 1066 CX Amsterdam, The Netherlands.
J Mol Diagn. 2010 Mar;12(2):238-43. doi: 10.2353/jmoldx.2010.090117. Epub 2010 Jan 21.
The classification of multifocal myxoid/round cell liposarcoma, which is defined as tumor presentation in at least two separate sites before manifestation in the lungs, as either metastasis or as a second primary tumor, has essential clinical consequences. Genetically, myxoid/round cell liposarcoma is characterized by t(12;16)(q13;p11) or t(12;22)(q13;q12), and various exon fusion transcripts are described with varying incidences, which permits their use as markers for clonality. Moreover, in solid tumors, analysis of loss of heterozygozity is valuable for clonality analysis. Therefore, fifteen multifocal myxoid/round cell liposarcoma patients with two to five metachronous (n = 12) or synchronous (n = 3) localizations were investigated. Using RT-PCR, the detailed molecular characteristics of the FUS-CHOP and EWS-CHOP breakpoints were determined. Loss of heterozygozity analysis at twelve loci was then used to further analyze clonal relationships. In all patients, tumor sites showed identical FUS-CHOP fusion products. In six patients, identical rare fusion transcripts were found, supporting a clonal relationship. Nine patients had the common exon5-FUS/exon2-CHOP fusion transcript, and two of these were identified as clonally related by loss of heterozygozity analysis. In all other patients, loss of heterozygozity analysis was highly suggestive of a clonal relationship, and no evidence for interpretation of a second primary tumor was found. This study supports the metastatic nature of apparent multifocal myxoid/round cell liposarcoma.
多灶性黏液样/圆细胞脂肪肉瘤的分类,定义为在肺部表现之前至少在两个不同部位出现的肿瘤表现,要么是转移瘤,要么是第二原发肿瘤,具有重要的临床意义。从遗传学上讲,黏液样/圆细胞脂肪肉瘤的特征是 t(12;16)(q13;p11) 或 t(12;22)(q13;q12),并且描述了各种外显子融合转录本,其发生率不同,因此可以用作克隆性标志物。此外,在实体肿瘤中,杂合性缺失分析对于克隆性分析很有价值。因此,对 15 例具有 2 至 5 个不同部位(n = 12)或同步(n = 3)局部定位的多灶性黏液样/圆细胞脂肪肉瘤患者进行了研究。使用 RT-PCR,确定了 FUS-CHOP 和 EWS-CHOP 断点的详细分子特征。然后使用 12 个位点的杂合性缺失分析进一步分析克隆关系。在所有患者中,肿瘤部位均显示出相同的 FUS-CHOP 融合产物。在 6 例患者中,发现了相同的罕见融合转录本,支持克隆关系。9 例患者具有常见的 exon5-FUS/exon2-CHOP 融合转录本,其中 2 例通过杂合性缺失分析被鉴定为克隆相关。在所有其他患者中,杂合性缺失分析高度提示克隆关系,并且没有发现第二个原发性肿瘤的解释证据。这项研究支持多灶性黏液样/圆细胞脂肪肉瘤的转移性本质。