Department of Dermatology, Gunma University Graduate School of Medicine, and Department of Pediatrics, Gunma Central General Hospital, Gunma, Japan.
Eur J Dermatol. 2010 Mar-Apr;20(2):208-10. doi: 10.1684/ejd.2010.0846. Epub 2010 Jan 28.
A 5-year-old girl presented with a two-month-history of skin rash and general fatigue. She had a slight fever, progressive muscle weakness and liver dysfunction. Gottron's papules on her fingers and purple-reddish papules on her elbows were noted. Serum aldolase levels were highly elevated, however, creatine phosphokinase levels were normal. An MRI revealed abnormal high signal changes in her gluteus minimus muscles. Interstitial pneumonia suddenly developed and she died despite aggressive treatment with methylprednisolone pulse therapy followed by intravenous administration of cyclophosphamide, immunoglobulin and cyclosporine A. Interstitial pneumonia is rare in juvenile dermatomyositis; however, as in adult cases, it can be fatal. In order to prevent severe complications and functional disabilities, early aggressive treatments should be considered when muscle inflammation is refractory to ordinary treatment.
一位 5 岁女孩因皮疹和全身乏力就诊,病史两个月。她有轻微发热、进行性肌无力和肝功能异常。手指有 Gottron 丘疹,肘部有紫红色丘疹。血清醛缩酶水平显著升高,而肌酸磷酸激酶水平正常。MRI 显示臀小肌异常高信号改变。并发间质性肺炎,尽管给予甲泼尼龙冲击治疗后序贯环磷酰胺、丙种球蛋白和环孢素 A 静脉输注,仍因病情恶化死亡。儿童皮肌炎中间质性肺炎罕见,但与成人病例一样,可能致命。为预防严重并发症和功能障碍,当肌肉炎症对常规治疗无反应时,应考虑早期积极治疗。