Rostásy K, Nagl A, Lütjen S, Roll K, Zotter S, Blaschek A, Korenke G C, Karenfort M, Gotwald T, Holthausen H
Department of Pediatrics IV, Division of Pediatric Neurology, Inherited Metabolic Disorders and Developmental Neurology, Medical University Innsbruck, Innsbruck, Austria.
Neuropediatrics. 2009 Oct;40(5):211-7. doi: 10.1055/s-0030-1247518. Epub 2010 Mar 10.
Acute disseminated encephalomyelitis (ADEM) is an acute, inflammatory-demyelinating disorder of the CNS with a favourable outcome in the majority of cases.
The aim of this study was to examine the long-term outcome of children with an initially severe form of ADEM.
Children with ADEM according to the criteria of the International Pediatric MS Study Group (IPMSSG) referred to the rehabilitation centre Vogtareuth were included. Neurological impairment was evaluated with a standardized telephone-based interview assessing the EDSS score. Neuropsychological outcome was assessed with review of the medical records and a standardized parental questionnaire (KOPKIJ).
Twelve children (1 year 9 months to 13 years of age) were included. All children had focal-neurological signs and changes in mental status at presentation and an MRI of the brain showing a range of white and gray matter lesions. 11/12 patients with a mean follow-up of 6.2 years (2-13.6 years) had a monophasic course of the disease. One child had a multiphasic ADEM. Two children had an EDSS score of 0, three an EDSS of 2, five an EDSS between 3 and 5 and two children had an EDSS score of 6 and 9. Results of a standardized parental questionnaire (KOPKIJ) revealed that 7 children had deficits in the categories alertness, memory, school performance, visual-spatial skills and/or impulse control.
The results of our study indicate that children with an initially severe manifestation of ADEM continue to have in the majority of cases neurological and neuropsychological handicaps.
急性播散性脑脊髓炎(ADEM)是一种中枢神经系统的急性炎症性脱髓鞘疾病,大多数病例预后良好。
本研究旨在探讨最初表现为重症形式的ADEM患儿的长期预后。
纳入符合国际儿童多发性硬化症研究组(IPMSSG)标准、转诊至Vogtareuth康复中心的ADEM患儿。通过基于电话的标准化访谈评估扩展残疾状态量表(EDSS)评分,以评估神经功能损害。通过查阅病历和标准化家长问卷(KOPKIJ)评估神经心理学预后。
纳入12名儿童(年龄1岁9个月至13岁)。所有儿童在就诊时均有局灶性神经体征和精神状态改变,脑部MRI显示一系列白质和灰质病变。11/12例平均随访6.2年(2 - 13.6年)的患者病程呈单相。1名儿童有多相性ADEM。2名儿童EDSS评分为0,3名评分为2,5名在3至5之间,2名儿童EDSS评分为6和9。标准化家长问卷(KOPKIJ)结果显示,7名儿童在警觉性、记忆力、学业表现、视觉空间技能和/或冲动控制方面存在缺陷。
我们的研究结果表明,最初表现为重症的ADEM患儿在大多数情况下仍存在神经和神经心理学障碍。