Bierich J R, Christie M, Heinrich J J, Martinez A S
Universitätskinderklinik Tübingen, Federal Republic of Germany.
Eur J Pediatr. 1991 Feb;150(4):246-9. doi: 10.1007/BF01955522.
Four children with severe congenital eye anomalies are described of which three had related symptoms. Two had bilateral anophthalmia, the optic nerves not detectable by computed cranial tomography and magnetic resonance imaging, and the third child had bilateral microphthalmia and coloboma iridis. The fourth patient had bilateral cryptophthalmia as part of Fraser syndrome. All four patients were of small stature. In three of them growth hormone deficiency was demonstrated which was of hypothalamic origin as shown by growth hormone releasing hormone tests. In the fourth child hypogonadotropic hypogonadism and tertiary thyroid deficiency were diagnosed which responded well to thyroxine treatment. Pathogenetically the described disorders are due to congenital defects of midline structures as a common "developmental field".
本文描述了4例患有严重先天性眼部异常的儿童,其中3例伴有相关症状。2例为双侧无眼球,计算机断层扫描和磁共振成像均未检测到视神经;第3例患儿为双侧小眼畸形和虹膜缺损。第4例患者患有双侧隐眼畸形,这是弗雷泽综合征的一部分。所有4例患者均身材矮小。其中3例显示生长激素缺乏,生长激素释放激素试验表明其起源于下丘脑。第4例患儿被诊断为低促性腺激素性性腺功能减退和三级甲状腺功能减退,对甲状腺素治疗反应良好。从发病机制上讲,所描述的疾病是由于中线结构作为一个共同的“发育区域”出现先天性缺陷所致。