Tanzer F, Buyukkayhan D, Cansu Mutlu E, Kalender Korkmaz F
Department of Pediatric Metabolism, Medical Faculty, Cumhuriyet University, Sivas, Turkey.
J Pediatr Endocrinol Metab. 2009 Dec;22(12):1159-62. doi: 10.1515/jpem.2009.22.12.1159.
Pompe's disease is a glycogen storage disease (type II) characterized by inherited autosomal recessive transmission. A 4 month-old girl presented with rapid disease progression, exhibiting severe hypotonia, and hypertrophic cardiomyopathy, progressing to respiratory failure by the age of 9 months. Despite its low incidence, infantile Pompe's disease is lethal. The availability of an effective treatment has created an urgent need to improve knowledge and early diagnosis of this disease. The clinical response is variable from patient to patient with a better effect in patients enrolled earlier. The only clinically available therapy for Pompe's disease is enzyme replacement therapy (ERT). Gene therapy is still not available for Pompe's disease due to lack of suitable vectors for long-term and tissue-specific expression. Recombinant human alpha-glucosidase remains a hope for patients.
庞贝氏病是一种糖原贮积病(II型),其特征为常染色体隐性遗传。一名4个月大的女孩疾病进展迅速,出现严重肌张力减退和肥厚型心肌病,9个月大时发展为呼吸衰竭。尽管发病率较低,但婴儿型庞贝氏病是致命的。有效治疗方法的出现迫切需要提高对这种疾病的认识和早期诊断。临床反应因患者而异,早期入组的患者效果更好。庞贝氏病唯一可临床应用的治疗方法是酶替代疗法(ERT)。由于缺乏用于长期和组织特异性表达的合适载体,基因疗法仍不适用于庞贝氏病。重组人α-葡萄糖苷酶仍是患者的希望。