Department of Neurosciences, University of Padova, Italy.
Curr Opin Pharmacol. 2010 Jun;10(3):338-45. doi: 10.1016/j.coph.2010.02.006. Epub 2010 Mar 29.
The recognition of a series of metabolic/enzymatic dysfunction in metabolic myopathies has allowed new therapeutic advances. The most recent ones are enzymatic replacement therapy (ERT) in glycogenosis type II in both the infantile, juvenile and the adult forms, targeted manipulation of diet that has been tried in glycogenosis type II (Pompe disease), type V (McArdle's disease), and in Carnitine palmitoyl transferase 2 (CPT 2) deficiency, a rare disorder of fatty acid oxidation. A well known hypolipidemic drug, bezafibrate, has been tested to stimulate expression of mutated gene for CPT 2, but it may represent a challenge for a series of other fatty acid mitochondrial disorders to restore the capacity for normal long-chain fatty oxidation in muscle. The present review summarizes the most recent clinical achievements that have achieved the interest for an accurate and early diagnosis of these metabolic disorders.
一系列代谢/酶功能障碍在代谢性肌病中的认识已经带来了新的治疗进展。最近的进展是糖原贮积症 II 型的酶替代疗法 (ERT),在婴儿型、青少年型和成人型中均有应用,以及针对糖原贮积症 II 型(庞贝病)、V 型(麦卡德尔病)和肉碱棕榈酰转移酶 2 (CPT 2) 缺乏症(一种罕见的脂肪酸氧化障碍)的饮食靶向治疗。一种著名的降脂药物贝扎贝特已被测试用于刺激 CPT 2 突变基因的表达,但对于一系列其他脂肪酸线粒体疾病来说,恢复肌肉中正常长链脂肪酸氧化的能力可能是一个挑战。本综述总结了最近的临床成就,这些成就引起了人们对这些代谢性疾病进行准确和早期诊断的兴趣。