Khalil Abdalla, Elhasid Ronit, Ben Barak Ayelet, Ben Arush Myriam Weyl
Department of Pediatric Hematology Oncology, Meyer Children's Hospital, Rambam Health Care Campus, Haifa, Israel.
Pediatr Hematol Oncol. 2010 Oct;27(7):574-80. doi: 10.3109/08880018.2010.493577.
The acquired form of pure red cell aplasia (PRCA) presents either as an acute self-limited disease, predominantly seen in children, or as a chronic illness more frequently seen in adults with rare spontaneous remissions. A 14-year-old boy presented with pallor, without hepatosplenomegaly, jaundice, lymphadenopathy, petechiae, or any other apparent abnormalities. Isolated anemia in the presence of normal white cell and platelet counts with a marrow of normal cellularity and absence of erythroblasts but normal myeloid cells and megakaryocytes revealed the diagnosis of PRCA. All possible investigations excluded secondary causes of PRCA. The patient required packed red cell transfusions every 2 to 3 weeks. He failed therapy with intravenous immunoglobulin, corticosteroids, cyclosporine A plus corticosteroids, antithymocyte globulin, anti-CD 20 (rituximab), and erythropoietin (EPO). He showed a severe, resistant, and transfusion-dependent PRCA. Spontaneous remission with normal hemoglobin and reticulocyte levels was dramatic 6.5 years after the diagnosis of PRCA and 3.6 years after his last treatment.
获得性纯红细胞再生障碍性贫血(PRCA)表现为急性自限性疾病,主要见于儿童,或为慢性疾病,更常见于成人,很少有自发缓解。一名14岁男孩出现面色苍白,无肝脾肿大、黄疸、淋巴结病、瘀点或任何其他明显异常。在白细胞和血小板计数正常、骨髓细胞正常、无成红细胞但髓细胞和巨核细胞正常的情况下出现单纯贫血,提示PRCA诊断。所有可能的检查均排除了PRCA的继发原因。该患者每2至3周需要输注浓缩红细胞。他接受静脉注射免疫球蛋白、皮质类固醇、环孢素A加皮质类固醇、抗胸腺细胞球蛋白、抗CD20(利妥昔单抗)和促红细胞生成素(EPO)治疗均无效。他表现为严重、难治且依赖输血的PRCA。在PRCA诊断6.5年后及最后一次治疗3.6年后,血红蛋白和网织红细胞水平恢复正常,出现了戏剧性的自发缓解。