Takahashi Kan, Oka Akira, Mizuguchi Masashi, Saitoh Makiko, Takita Junko, Sato Atsushi, Mimaki Masakazu, Kato Motohiro, Ogawa Seishi, Igarashi Takashi
Department of Pediatrics, Graduate School of Medicine, the University of Tokyo, 7-3-1 Hongo, Bunkyo-ku, Tokyo, Japan.
Brain Dev. 2011 Apr;33(4):353-6. doi: 10.1016/j.braindev.2010.06.014. Epub 2010 Aug 21.
A patient with a large deletion of the distal part of the long arm of chromosome 13 showed severe psychomotor retardation, a characteristic face, nystagmus, retinopathy, cystic kidney disease, and brain malformation with molar tooth sign and cerebellar vermis hypoplasia, a phenotype typical of Arima syndrome. This patient also had bilateral retinoblastoma. Fluorescent in situ hybridization and single-nucleotide-polymorphism genotyping microarray demonstrated an interstitial deletion of 54 Mbp, ranging from 13q14.13 to 13q32.3 and involving the RB1 gene. This patient is the first case of Arima syndrome, or a Joubert syndrome-related disorder, that showed linkage to chromosome 13q.