Forrest Katharine M, Siddiqui Ata, Lim Ming, Wraige Elizabeth
Department of Paediatric Neurology, Southampton General Hospital, Southampton, UK.
Childs Nerv Syst. 2011 Jan;27(1):193-6. doi: 10.1007/s00381-010-1267-y. Epub 2010 Aug 28.
Dolichoectasia describes the elongation, dilatation and tortuosity of an arterial vessel. In adults, clinical presentation of basilar dolichoectasia (BD) is most often with ischaemic stroke. True BD has been very rarely reported in childhood, but the implication is of a congenital susceptibility.
We describe two cases of infants with BD complicated by brainstem ischaemia.
This first description of childhood BD associated with ischaemic infarction adds to the understanding of this rarely reported arteriopathy.
动脉扩张迂曲是指动脉血管的延长、扩张和迂曲。在成年人中,基底动脉扩张迂曲(BD)的临床表现最常见的是缺血性中风。儿童期真正的BD非常罕见,但这意味着先天性易感性。
我们描述了两例患有BD并伴有脑干缺血的婴儿病例。
这首次对与缺血性梗死相关的儿童期BD的描述,增进了我们对这种罕见动脉病的理解。