Pediatric Urology Research Center, Department of Pediatric Urology, Children's Hospital Medical Center, Tehran University of Medical Sciences, Tehran, Iran.
Urology. 2011 Jul;78(1):186-8. doi: 10.1016/j.urology.2010.09.019. Epub 2010 Dec 4.
To present the case of a 5-day-old male infant referred to our clinic with complaints of huge swollen testes, recurrent urinary tract infection, and diarrhea. The imaging studies and surgical assessments revealed a urethrorectal fistula and 2 nonfunctional urethras. Cutaneous vesicostomy was performed urgently to avoid additional renal infection. At the age of 6 months, the anterior anal insertion was repaired by perineal access. Eventually, urethral reconstruction was performed when the boy was 3 years old. The patient was asymptomatic at the last follow-up examination without additional urinary tract infections. The combination of urethrovasal reflux and congenital urethral triplication, consisting of urethrorectal fistula, has not been previously reported.
现报告 1 例 5 日龄男婴,因睾丸巨大肿胀、反复尿路感染和腹泻就诊。影像学检查和手术评估显示存在尿道直肠瘘和 2 条无功能尿道。紧急行皮膚膀胱造口术以避免肾脏进一步感染。6 个月大时,经会阴入路修复前肛门插入。最终,男孩 3 岁时进行了尿道重建。最后一次随访时患者无症状,无额外尿路感染。尿道- 尿道窦反流和先天性尿道三重性(包括尿道直肠瘘)的组合此前尚未报道过。