Institute of Biochemistry and Clinical Biochemistry, Catholic University of Rome Sacro Cuore, Largo F. Vito 1, 00164, Rome, Italy.
Mol Cell Biochem. 2012 Jan;359(1-2):205-16. doi: 10.1007/s11010-011-1015-y. Epub 2011 Aug 12.
Physiologic concentration in amniotic fluid (AF) of several metabolites has not been established with certainty. In this study, we initially assayed purines, pyrimidines, and amino compounds in 1,257 AF withdrawn between the 15th and the 20th week of gestation from actually normal pregnancies (normal gestations, normal offspring). Results allowed to determine physiologic reference intervals for 45 compounds. In these AF, not all purines and pyrimidines were detectable and uric acid (238.35±76.31 μmol/l) had the highest concentration. All amino compounds were measurable, with alanine having the highest concentration (401.10±88.47 μmol/l). In the second part of the study, we performed a blind metabolic screening of AF to evaluate the utility of this biochemical analysis as an additional test in amniocenteses. In 1,295 additional AF from normal pregnancies, all metabolites fell within the confidence intervals determined in the first part of the study. In 24 additional AF from women carrying Down's syndrome-affected fetuses, glutamate, glutamine, glycine, taurine, valine, isoleucine, leucine, ornithine, and lysine were different from physiologic reference values. One AF sample showed phenylalanine level of 375.54 μmol/l (mean value in normal AF=65.07 μmol/l) and was from a woman with unreported phenylketonuria with mild hyperphenylalaninemia (serum phenylalanine=360.88 μmol/l), carrying the IVS 4+5 G-T and D394A mutations. The fetus was heterozygote for the maternal D394A mutation. An appropriate diet maintained the mother phenylalanine in the range of normality during pregnancy, avoiding serious damage in fetal and neonatal development. These results suggest that the metabolic screening of AF might be considered as an additional biochemical test in amniocenteses useful to highlight anomalies potentially related to IEM.
羊水(AF)中几种代谢物的生理浓度尚未得到明确确定。在这项研究中,我们最初测定了 15 至 20 孕周正常妊娠(正常妊娠,正常胎儿)的 1257 份羊水样本中的嘌呤、嘧啶和氨基酸化合物。结果确定了 45 种化合物的生理参考区间。在这些羊水样本中,并非所有嘌呤和嘧啶都可检测到,尿酸(238.35±76.31 μmol/l)的浓度最高。所有氨基酸化合物均可测量,其中丙氨酸浓度最高(401.10±88.47 μmol/l)。在研究的第二部分,我们对羊水进行了盲代谢筛查,以评估这种生化分析作为羊膜穿刺术的附加检测的效用。在 1295 份来自正常妊娠的额外羊水样本中,所有代谢物均在研究第一部分确定的置信区间内。在 24 份来自携带唐氏综合征胎儿的女性的额外羊水样本中,谷氨酸、谷氨酰胺、甘氨酸、牛磺酸、缬氨酸、异亮氨酸、亮氨酸、鸟氨酸和赖氨酸与生理参考值不同。一份羊水样本显示苯丙氨酸水平为 375.54 μmol/l(正常羊水的平均值=65.07 μmol/l),来自一名未报告有轻度高苯丙氨酸血症的苯丙酮尿症患者(血清苯丙氨酸=360.88 μmol/l),携带 IVS 4+5 G-T 和 D394A 突变。胎儿为母亲 D394A 突变的杂合子。适当的饮食使母亲在怀孕期间的苯丙氨酸保持在正常范围内,避免了胎儿和新生儿发育的严重损害。这些结果表明,羊水的代谢筛查可以作为羊膜穿刺术的附加生化检测,有助于突出与 IEM 相关的潜在异常。