Zhang Xin-shun, Zhang Hui-wen, Gu Xue-fan
-Shanghai Jiaotong University School of Medicine, Shanghai Institute for Pediatric Research, Shanghai, People's Republic of China.
Zhonghua Yi Xue Yi Chuan Xue Za Zhi. 2011 Oct;28(5):536-8. doi: 10.3760/cma.j.issn.1003-9406.2011.05.014.
To establish a method of iduronate-2-sulfatase (IDS) activity assay and mutation analysis of IDS gene for the prenatal diagnosis of mucopolysaccharidosis type II (MPSII).
Prenatal diagnosis of two cases was performed using cultured fetal amniotic fluid cells. Enzyme activity of IDS in cultured fetal amniotic fluid cells extracted from the two pregnant women at high risk of MPS II was measured. Meanwhile, genomic DNA was extracted for fetal gender testing and mutation analysis of the IDS gene.
Enzyme activity assay showed that IDS activity in amniotic fluid cells was significantly decreased. IDS gene sequencing showed that the male fetus was hemizygous mutant, and the female fetus was carrier of heterozygous mutation. Therefore the male fetus was an MPS II patient and the female fetus was a mutation carrier.
Determination of IDS activity in fetal amniotic fluid cells together with IDS gene mutation analysis is a rapid, sensitive and accurate method of prenatal diagnosis of MPS II. Using this method, prenatal diagnosis for pregnant women at high risk of MPSII can be achieved.
建立艾杜糖醛酸-2-硫酸酯酶(IDS)活性检测及IDS基因突变分析方法,用于Ⅱ型黏多糖贮积症(MPSII)的产前诊断。
采用培养的胎儿羊水细胞对2例进行产前诊断。检测从2例MPS II高危孕妇提取的培养胎儿羊水细胞中IDS的酶活性。同时,提取基因组DNA进行胎儿性别检测及IDS基因突变分析。
酶活性检测显示羊水细胞中IDS活性显著降低。IDS基因测序显示男性胎儿为半合子突变,女性胎儿为杂合子突变携带者。因此,男性胎儿为MPS II患者,女性胎儿为突变携带者。
检测胎儿羊水细胞中的IDS活性并结合IDS基因突变分析是一种快速、灵敏且准确的MPS II产前诊断方法。采用该方法可对MPSII高危孕妇进行产前诊断。