Université de Bordeaux, Biothérapies des Maladies Génétiques et Cancers, U1035, F-33000 Bordeaux, France.
IUBMB Life. 2011 Nov;63(11):979-86. doi: 10.1002/iub.529. Epub 2011 Oct 14.
Glycogen storage disease type II or Pompe disease (GSD II, MIM 232300) is a rare inherited metabolic myopathy caused by a deficiency of lysosomal acid α-glucosidase or acid maltase (GAA; EC 3.2.1.20), resulting in a massive lysosomal glycogen accumulation in cardiac and skeletal muscles. Affected individuals exhibit either severe hypotonia associated with hypertrophic cardiomyopathy (infantile forms) or progressive muscle weakness (late-onset forms). Even if enzyme replacement therapy has recently become a standard treatment, it suffers from several limitations. This review will present the main results of enzyme replacement therapy and the recent findings concerning alternative treatments for Pompe disease, such as gene therapy, enzyme enhancement therapy, and substrate reduction therapy.
糖原贮积病 II 型或庞贝病(GSD II,MIM 232300)是一种罕见的遗传性代谢性肌病,由溶酶体酸性α-葡萄糖苷酶或酸性麦芽糖酶(GAA;EC 3.2.1.20)缺乏引起,导致心脏和骨骼肌中大量溶酶体糖原积累。受影响的个体表现出严重的低张力,伴有肥厚型心肌病(婴儿型)或进行性肌肉无力(迟发型)。尽管酶替代疗法最近已成为一种标准治疗方法,但它存在一些局限性。本综述将介绍酶替代疗法的主要结果以及关于庞贝病的替代治疗方法的最新发现,如基因治疗、酶增强疗法和底物减少疗法。