Cardiovascular Institute, University of Pittsburgh, Pittsburgh, PA 15213, USA.
Hum Gene Ther. 2012 Jul;23(7):722-32. doi: 10.1089/hum.2011.108. Epub 2012 Jul 11.
The calcium pump SERCA2a (sarcoplasmic reticulum calcium ATPase 2a), which plays a central role in cardiac contraction, shows decreased expression in heart failure (HF). Increasing SERCA2a expression in HF models improves cardiac function. We used direct cardiac delivery of adeno-associated virus encoding human SERCA2a (AAV6-hSERCA2a) in HF and normal canine models to study safety, efficacy, and the effects of immunosuppression. Tachycardic-paced dogs received left ventricle (LV) wall injection of AAV6-hSERCA2a or solvent. Pacing continued postinjection for 2 or 6 weeks, until euthanasia. Tissue/serum samples were analyzed for hSERCA2a expression (Western blot) and immune responses (histology and AAV6-neutralizing antibodies). Nonpaced dogs received AAV6-hSERCA2a and were analyzed at 12 weeks; a parallel cohort received AAV-hSERCA2a and immunosuppression. AAV-mediated cardiac expression of hSERCA2a peaked at 2 weeks and then declined (to ~50%; p<0.03, 6 vs. 2 weeks). LV end diastolic and end systolic diameters decreased in 6-week dogs treated with AAV6-hSERCA2a (p<0.05) whereas LV diameters increased in control dogs. Dogs receiving AAV6-hSERCA2a developed neutralizing antibodies (titer ≥1:120) and cardiac cellular infiltration. Immunosuppression dramatically reduced immune responses (reduced inflammation and neutralizing antibody titers <1:20), and maintained hSERCA2a expression. Thus cardiac injection of AAV6-hSERCA2a promotes local hSERCA2a expression and improves cardiac function. However, the hSERCA2a protein level is reduced by host immune responses. Immunosuppression alleviates immune responses and sustains transgene expression, and may be an important adjuvant for clinical gene therapy trials.
肌浆网钙 ATP 酶 2a(SERCA2a)是心脏收缩的核心,在心力衰竭(HF)中表达减少。在 HF 模型中增加 SERCA2a 的表达可改善心脏功能。我们使用腺相关病毒(AAV)编码的人类 SERCA2a(AAV6-hSERCA2a)直接心脏传递,在 HF 和正常犬模型中研究安全性、疗效和免疫抑制的影响。心动过速起搏犬接受左心室(LV)壁注射 AAV6-hSERCA2a 或溶剂。注射后继续起搏 2 或 6 周,直到安乐死。分析组织/血清样本以检测 hSERCA2a 表达(Western blot)和免疫反应(组织学和 AAV6 中和抗体)。非起搏犬接受 AAV6-hSERCA2a 治疗,并在 12 周时进行分析;平行队列接受 AAV-hSERCA2a 和免疫抑制。AAV 介导的 hSERCA2a 在心脏中的表达在 2 周时达到峰值,然后下降(至~50%;p<0.03,6 周比 2 周)。接受 AAV6-hSERCA2a 治疗的 6 周犬的 LV 舒张末期和收缩末期直径减小(p<0.05),而对照犬的 LV 直径增加。接受 AAV6-hSERCA2a 治疗的犬产生中和抗体(滴度≥1:120)和心脏细胞浸润。免疫抑制显著降低免疫反应(减少炎症和中和抗体滴度<1:20),并维持 hSERCA2a 表达。因此,AAV6-hSERCA2a 的心脏注射可促进局部 hSERCA2a 表达并改善心脏功能。然而,宿主免疫反应会降低 hSERCA2a 蛋白水平。免疫抑制减轻免疫反应并维持转基因表达,可能是临床基因治疗试验的重要辅助手段。