Suppr超能文献

发作性睡病的发病机制:从HLA关联到下丘脑泌素缺乏

[Pathogenesis of narcolepsy: from HLA association to hypocretin deficiency].

作者信息

Klein G, Burghaus L, Diederich N

机构信息

Klinik I für Innere Medizin, Universitätsklinikum Köln, Köln, Germany.

出版信息

Fortschr Neurol Psychiatr. 2012 Nov;80(11):627-34. doi: 10.1055/s-0031-1299447. Epub 2012 Jun 13.

Abstract

Narcolepsy is a rare and chronic sleep disorder, characterised by excessive daytime sleepiness. Frequently associated signs are cataplexy, sleep paralysis and hypnagogic or hypnopompic hallucinations. Advances in understanding the pathogenesis of the disease have essentially been elucidated during the last fifteen years. The most significant finding has been the discovery of hypocretin-1 and -2 in 1998. Hypocretin-containing cells have widespread projections throughout the entire CNS and play a crucial role in the regulation of the sleep-wake cycle. They also contribute to olefaction and to the regulation of food intake. Animal models and human studies concordantly show that the disturbed hypocretin system is the probable cause of narcolepsy. However, it remains unclear why there is neuronal death of hypocretin-producing cells in the lateral hypothalamus. As the HLA-allele DQB1*0602 is associated with narcolepsy and hypocretin deficiency, an autoimmune reaction against hypocretin-producing neurons has been vigorously discussed. Newly discovered gene polymorphisms as well as previously unknown pathogenetic mechanisms, linking the sleep-wake cycle with the immune system, may also contribute to the pathogenetic cascade. Worthy of mention in this context is, e.g., the "insulin-like growth factor"-binding protein 3 (IGFBP3), whose overexpression causes a down-regulation of the hypocretin production. Substitution of the deficient neuropeptides by hypocretin agonists may become the causal treatment strategy of the future, if an adequate administration route can be found. Presently, animal trials, including genetic therapy, cell transplantations or the administration of hypocretin receptor agonists, are underway.

摘要

发作性睡病是一种罕见的慢性睡眠障碍,其特征为日间过度嗜睡。常见的相关症状有猝倒、睡眠瘫痪以及入睡或觉醒时的幻觉。在过去十五年中,对该疾病发病机制的理解取得了实质性进展。最重大的发现是1998年发现了下丘脑泌素-1和-2。含下丘脑泌素的细胞在整个中枢神经系统有广泛投射,在睡眠-觉醒周期的调节中起关键作用。它们还参与嗅觉和食物摄入的调节。动物模型和人体研究一致表明,下丘脑泌素系统紊乱可能是发作性睡病的病因。然而,尚不清楚为什么下丘脑外侧产生下丘脑泌素的细胞会发生神经元死亡。由于HLA等位基因DQB1*0602与发作性睡病和下丘脑泌素缺乏有关,针对产生下丘脑泌素的神经元的自身免疫反应一直是激烈讨论的焦点。新发现的基因多态性以及将睡眠-觉醒周期与免疫系统联系起来的先前未知的发病机制,也可能促成发病过程。在这方面值得一提的是,例如“胰岛素样生长因子”结合蛋白3(IGFBP3),其过度表达会导致下丘脑泌素产生的下调。如果能找到合适的给药途径,用下丘脑泌素激动剂替代缺乏的神经肽可能成为未来的病因治疗策略。目前,包括基因治疗、细胞移植或下丘脑泌素受体激动剂给药在内的动物试验正在进行中。

文献检索

告别复杂PubMed语法,用中文像聊天一样搜索,搜遍4000万医学文献。AI智能推荐,让科研检索更轻松。

立即免费搜索

文件翻译

保留排版,准确专业,支持PDF/Word/PPT等文件格式,支持 12+语言互译。

免费翻译文档

深度研究

AI帮你快速写综述,25分钟生成高质量综述,智能提取关键信息,辅助科研写作。

立即免费体验