复发性右侧舌下腺囊肿，伴同侧下颌下腺发育不全。
Recurrent right sublingual ranula, concomitant with ipsilateral submandibular salivary gland aplasia.
作者信息
Albsoul Nader M, Obeidat Fatima O, Altaher Raed N, Jubouri Shams A, Hadidy Azmy M
机构信息
Department of Surgery, Division of Head & Neck Surgery, University Of Jordan Hospital, Faculty of Medicine, Amman, Jordan.
出版信息
Int J Surg Case Rep. 2013;4(2):229-31. doi: 10.1016/j.ijscr.2012.10.021. Epub 2012 Dec 1.
INTRODUCTION
Oral ranula is a retention cyst that arises from the salivary gland with recurrence rate of up to 25% after complete excision of ranula and up to 2% in case of complete excision of ranula and sublingual gland. Major salivary gland aplasia is a rare finding that is usually associated with other developmental anomalies.
PRESENTATION OF CASE
We report a 15-year-old female patient presented with recurrent intraoral cystic swelling that was documented to be sublingual ranula. CT scan revealed also the absence of right submandibular salivary gland with persistence of its Whartons duct. This combination has never been reported previously.
DISCUSSION
The combination of recurrent sublingual ranula associated with aplasia of ipsilateral submandibular salivary gland and persistence of Whartons duct has never been reported before in the literature, a finding that may provide the base for future research.
CONCLUSION
Further research may prove similar associations between oral ranula and salivary gland aplasia, which may have clinical implications on diagnostic and management plan decisions.
引言
口腔黏液囊肿是一种潴留性囊肿，起源于唾液腺，黏液囊肿完全切除术后复发率高达25%，黏液囊肿及舌下腺完全切除术后复发率高达2%。主要唾液腺发育不全是一种罕见的表现，通常与其他发育异常有关。
病例介绍
我们报告一名15岁女性患者，表现为复发性口腔内囊性肿胀，经诊断为舌下黏液囊肿。CT扫描还显示右侧下颌下唾液腺缺如，但其沃顿管持续存在。这种组合此前从未有过报道。
讨论
复发性舌下黏液囊肿合并同侧下颌下唾液腺发育不全及沃顿管持续存在，这一组合在文献中此前从未有过报道，这一发现可能为未来的研究提供基础。
结论
进一步的研究可能会证实口腔黏液囊肿与唾液腺发育不全之间存在类似的关联，这可能对诊断和治疗方案的决策具有临床意义。
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