Hogan A M, Mannion M, Ryan R S, Khan W, Waldron R, Barry K
Department of Surgery, Mayo General Hospital, Castlebar, Co. Mayo, Ireland; Department of Radiology, Mayo General Hospital, Castlebar, Co. Mayo, Ireland.
Int J Surg Case Rep. 2013;4(3):299-301. doi: 10.1016/j.ijscr.2012.08.005. Epub 2012 Sep 1.
Ischiorectal abscesses have been shown to form sinuses with various deep structures but continuity with the spinal canal is extremely rare.
A previously healthy sixty-five year old man presented emergently with rectal pain, weight loss and recurrent severe tension headaches. He had systemic sepsis and resultant coagulapathy (INR 3.4) which precluded investigation of neurological symptoms by lumbar puncture. MRI rectum demonstrated a well circumscribed fluid collection with direct connection to the spinal canal and containing meningeal tissue. It extended inferiorly to the right ischiorectal fossa and abutted the natal cleft. A radiological diagnosis of ischiorectal abscess which had become continuous with a previously existing anterior sacral myelomeningocoele (ASM) was made. He was treated with broad spectrum antibiotics and a neurosurgical opinion was sought. He remained clinically unwell (septic and coagulopathic) until the abscess fistulated through the perianal skin, draining pus mixed with clear fluid (likely CSF) at which point he improved systemically.
Few general surgeons would be faced with acute management of complicated ASM. Paucity of literature made application of evidence based medicine difficult. In fit healthy patients surgery is the mainstay of treatment as myelomengingoceles do not regress spontaneously. Conservative management is associated with up to 30% mortality (largely due to bacterial meningitis). The patient in this case was adamant that he did not consent to definitive surgical intervention.
This case highlights challenges encountered in the management of complicated ASM in a general hospital.
坐骨直肠窝脓肿已被证实可与各种深部结构形成窦道,但与椎管相通极为罕见。
一名65岁既往健康的男性因直肠疼痛、体重减轻和反复出现的严重紧张性头痛紧急就诊。他患有全身性脓毒症及由此导致的凝血功能障碍(国际标准化比值3.4),这使得通过腰椎穿刺对神经症状进行检查受到限制。直肠磁共振成像显示有一个边界清晰的液性聚集区,与椎管直接相连且包含脑膜组织。它向下延伸至右侧坐骨直肠窝并毗邻臀裂。经放射学诊断为坐骨直肠窝脓肿,该脓肿已与先前存在的骶前脊髓脊膜膨出(ASM)相通。给予他广谱抗生素治疗,并寻求神经外科会诊意见。在脓肿经肛周皮肤形成瘘管,引出混有清亮液体(可能为脑脊液)的脓液之前,他的临床状况一直不佳(脓毒症和凝血功能障碍),此时他的全身状况有所改善。
很少有普通外科医生会面临复杂ASM的急性处理情况。文献资料匮乏使得应用循证医学变得困难。对于健康状况良好的患者,手术是主要的治疗方法,因为脊髓脊膜膨出不会自行消退。保守治疗的死亡率高达30%(主要由于细菌性脑膜炎)。该病例中的患者坚决不同意进行确定性手术干预。
本病例突出了综合医院在处理复杂ASM时所遇到的挑战。