Department of Pediatrics, USC Keck School of Medicine & Childrens Hospital Los Angeles, Los Angeles, CA 90033, USA.
Dev Biol. 2013 Jun 1;378(1):13-24. doi: 10.1016/j.ydbio.2013.03.018. Epub 2013 Apr 3.
Wnt signaling is critical for cell fate specification and cell differentiation in many organs, but its function in pulmonary neuroendocrine cell (PNEC) differentiation has not been fully addressed. In this study, we examined the role of canonical Wnt signaling by targeting the gene for Adenomatous Polyposis Coli (Apc), which controls Wnt signaling activity via mediating phosphorylation of beta-catenin (Ctnnb). Targeting the Apc gene in lung epithelial progenitors by Nkx2.1-cre stabilized Ctnnb and activated canonical Wnt signaling. Apc deficiency altered lung epithelial cell fate by inhibiting Clara and ciliated cell differentiation and activating Uchl1, a marker of neuroendocrine cells. Similar to PNEC in normal lung, Uchl1(positive) cells were innervated. In mice with targeted inactivation of Ctnnb by Nkx2.1-cre, PNEC differentiation was not interrupted. These indicate that, after lung primordium formation, Wnt signaling is not essential for PNEC differentiation; however, its over-activation promotes PNEC features. Interestingly, Nkx2.1 was extinguished in Apc deficient epithelial progenitors before activation of Uchl1. Examination of Nkx2.1 null lungs suggested that early deletion of Nkx2.1 inhibits PNEC differentiation, while late repression does not. Nkx2.1 was specifically inhibited in Apc deficient lungs but not in Ctnnb gain-of-function lungs indicating a functional difference between Apc deletion and Ctnnb stabilization, both of which activate Wnt signaling. Further analysis revealed that Apc deficiency led to increased TGF-beta signaling, which inhibited Nkx2.1 in cultured lung endodermal explants. In contrast, TGF-beta activity was not increased in Ctnnb gain-of-function lungs. Therefore, our studies revealed an important mechanism involving Apc and TGF-beta signaling in regulating the key transcriptional factor, Nkx2.1, for lung epithelial progenitor cell fate determination.
Wnt 信号通路对于许多器官中的细胞命运特化和细胞分化至关重要,但它在肺神经内分泌细胞 (PNEC) 分化中的功能尚未完全阐明。在这项研究中,我们通过靶向 APC 基因(通过调节β-连环蛋白 (Ctnnb) 的磷酸化来控制 Wnt 信号活性)来研究经典 Wnt 信号通路的作用。在肺上皮祖细胞中靶向 Nkx2.1-cre 稳定 Ctnnb 并激活经典 Wnt 信号通路。Apc 缺陷通过抑制 Clara 和纤毛细胞分化并激活 Uchl1(神经内分泌细胞的标志物)来改变肺上皮细胞命运。与正常肺中的 PNEC 相似,Uchl1(+)细胞被神经支配。在 Nkx2.1-cre 靶向失活 Ctnnb 的小鼠中,PNEC 分化未被中断。这表明,在肺原基形成后,Wnt 信号对于 PNEC 分化不是必需的;然而,其过度激活促进了 PNEC 的特征。有趣的是,在 Uchl1 激活之前,Apc 缺陷的上皮祖细胞中 Nkx2.1 被熄灭。对 Nkx2.1 缺失肺的检查表明,早期缺失 Nkx2.1 抑制 PNEC 分化,而晚期抑制则不抑制。Nkx2.1 仅在 Apc 缺陷的肺中被特异性抑制,而不在 Ctnnb 功能获得的肺中被抑制,这表明 Apc 缺失和 Ctnnb 稳定之间存在功能差异,两者都激活了 Wnt 信号通路。进一步分析表明,Apc 缺陷导致 TGF-β信号增加,从而抑制培养的肺内胚层外植体中的 Nkx2.1。相比之下,在 Ctnnb 功能获得的肺中,TGF-β活性并未增加。因此,我们的研究揭示了涉及 Apc 和 TGF-β信号通路的重要机制,该机制调节了肺上皮祖细胞命运决定的关键转录因子 Nkx2.1。