Keppen L D, Brodsky M C, Michael J M, Poindexter A R
Department of Pediatrics, University of Arkansas for Medical Sciences, Little Rock.
Am J Med Genet. 1990 Jul;36(3):285-7. doi: 10.1002/ajmg.1320360307.
Five of 13 patients with microphthalmia or clinical anophthalmia studied in an institution of 650 mentally retarded adults had hypogonadotropic hypogonadism. Four males had low testosterone levels and sexual infantilism, manifesting as micropenis with small testes or cryptorchidism. One female had primary amenorrhea. All 5 patients had low gonadotropin levels, confirming a hypothalamic or pituitary basis for their hypogonadism. Thyroxin, thyroid stimulating hormone, prolactin, and A.M. cortisol were also measured and were normal. All patients with hypogonadotropic hypogonadism were chromosomally normal and had variable central nervous system defects, suggesting that they comprise a heterogeneous group of disorders. Microphthalmia or anophthalmia in a mentally retarded patient is associated with hypogonadotropic hypogonadism.
在一所拥有650名成年智障患者的机构中,对13例小眼症或临床无眼症患者进行研究,其中5例患有低促性腺激素性性腺功能减退。4名男性睾酮水平低且有性幼稚症,表现为阴茎短小、睾丸小或隐睾。1名女性有原发性闭经。所有5例患者促性腺激素水平均低,证实其性腺功能减退为下丘脑或垂体原因所致。还检测了甲状腺素、促甲状腺激素、催乳素和上午皮质醇水平,结果均正常。所有低促性腺激素性性腺功能减退患者染色体均正常,并有不同程度的中枢神经系统缺陷,提示这是一组异质性疾病。智障患者中的小眼症或无眼症与低促性腺激素性性腺功能减退有关。