Instituto de Medicina Molecular, Faculdade de Medicina da Universidade de Lisboa, Lisboa, Portugal Instituto Gulbenkian de Ciência, Oeiras, Portugal.
Rheumatology Research Center, Shariati Hospital, Tehran University of Medical Sciences, Tehran, Iran.
Ann Rheum Dis. 2015 Mar;74(3):618-24. doi: 10.1136/annrheumdis-2013-204475. Epub 2013 Dec 10.
To identify new susceptibility loci for Behçet's disease (BD), we performed a genome-wide association study (GWAS) using DNA pooling.
Two replicate pools of 292 Iranian BD cases and of 294 age- and sex-matched controls were allelotyped in quadruplicate on the Affymetrix Genome-Wide Human SNP Array 6.0. Of the 51 top markers, 47 were technically validated through individually genotyping. Replication of validated single nucleotide polymorphisms (SNPs) was performed in an independent Iranian dataset (684 cases and 532 controls).
In addition to the well-established HLA-B locus, rs7528842 in a gene desert on chromosome 1p21.2, and rs632111 at the 3'UTR of FUT2 were associated in both the discovery and replication datasets (individually and in combination). However, only the FUT2 SNP was associated in a previous GWAS for BD in Turkish people. Fine-mapping of FUT2 in the full Iranian dataset showed additional associations in five coding SNPs (2.97E-06<pcombined<1.34E-04), including the rs601338 nonsense (W143X) variant which, in Caucasians, determines the secretion of the H antigen (precursor of the ABO blood group antigens) in body fluids and on the intestinal mucosa. Meta-analysis with the published Turkish GWAS data strengthened the FUT2 associations (4.78E-09<pmeta<1.66E-07).
This study suggests for the first time a putative link between a specific gene and environment in the aetiopathogenesis of BD. The non-secretor phenotype affects mucosal glycosylation, which may explain its known association with dysbiosis and altered susceptibility to infections. A different antigenic stimulation in early life and consequent increased propensity for autoimmunity and inflammation may contribute to BD development.
为了确定白塞病(BD)的新易感基因座,我们使用 DNA 池进行了全基因组关联研究(GWAS)。
我们对 292 名伊朗 BD 患者和 294 名年龄和性别匹配的对照者进行了两次重复 DNA 池的全基因组 SNP 芯片(Affymetrix Genome-Wide Human SNP Array 6.0)基因分型,在 51 个最显著的标记物中,有 47 个通过个体基因分型进行了技术验证。在独立的伊朗数据集(684 例病例和 532 例对照者)中对验证的单核苷酸多态性(SNP)进行了重复验证。
除了已确立的 HLA-B 基因座外,染色体 1p21.2 上的基因荒漠中的 rs7528842 和 FUT2 3'UTR 中的 rs632111 在发现和复制数据集(单独和组合)中均存在关联。然而,在土耳其人的先前的 BD GWAS 中,只有 FUT2 SNP 存在关联。在全伊朗数据集的 FUT2 精细定位中,在五个编码 SNP 中发现了其他关联(2.97E-06<pcombined<1.34E-04),包括无义突变(W143X)变体 rs601338,在白种人中,该变体决定了体液和肠黏膜上 H 抗原(ABO 血型抗原的前体)的分泌。与已发表的土耳其 GWAS 数据的荟萃分析加强了 FUT2 关联(4.78E-09<pmeta<1.66E-07)。
本研究首次提示特定基因与 BD 发病机制中的特定环境之间可能存在关联。非分泌表型影响粘膜糖基化,这可能解释其与微生态失调和易感性改变相关的已知关联。在生命早期的不同抗原刺激和随后的自身免疫和炎症倾向增加可能导致 BD 的发生。