婴儿牙源性黏液瘤：一种特殊的实体。

Infant Odontogenic Myxoma: a specific entity.

作者信息

Kadlub Natacha, Mbou Valere Belle, Leboulanger Nicolas, Lepointe Hubert Ducou, Ansari Edward, L'hermine Aurore Coulomb, Davrou Julien, Vazquez Marie-Paule, Picard Arnaud

机构信息

APHP (Head: Prof. Vazquez), Hôpital Necker Enfants Malades, Service de chirurgie Maxillofaciale, Paris 75015, France; Université Paris V, UFR de Médecine Paris Descartes, Paris 75006, France; Centre de références des malformations de la face et de la cavité buccale (Head: Prof. Vazquez), Paris 75015, France; Laboratoire de Physiopathologie orale et Moléculaire (Head: Prof. Berdal), INSERM, UMRS 872, Equipe 5, Centre de recherche des Cordeliers, Paris 75006, France.

APHP (Head: Prof. Coulomb L'Herminé), Hôpital Armand Trousseau, Service de cytologie et anatomopathologie, Paris 75012, France.

出版信息

J Craniomaxillofac Surg. 2014 Dec;42(8):2082-6. doi: 10.1016/j.jcms.2013.07.019. Epub 2014 Jan 12.

DOI:10.1016/j.jcms.2013.07.019

PMID:24429059

Abstract

INTRODUCTION

In children, and specifically in infants, odontogenic myxomas are extremely rare. In infants, myxoma seems to display mostly the same clinical, radiological and pathological characteristics. This paper presents a series of odontogenic myxomas in infant patients.

MATERIALS AND METHODS

Four infant patients were included in this retrospective study. The clinical, radiological and pathological presentation was characterized and the treatment analysed.

RESULTS

All patients presented with a rapidly evolving paranasal swelling. CT-scan showed a maxillary homogeneous unilocular and intraosseous tumour. In all cases, pathological examination revealed a loose myxoid stroma within stellate and spindle shaped cells. All patients underwent conservative surgery through a vestibular approach.

CONCLUSION

This patient series and a review of the literature demonstrates that odontogenic myxoma is specific in infant. We propose the name of Infant Odontogenic Myxoma for this entity.

摘要