Diaz-Chico J C, Yang K G, Stoming T A, Efremov D G, Kutlar A, Kutlar F, Aksoy M, Altay C, Gurgey A, Kilinc Y
Department of Cell and Molecular Biology, Medical College of Georgia, Augusta 30912-3331.
Blood. 1988 Jan;71(1):248-51.
Through the procedure of gene amplification combined with hybridization to synthetic 19 base pair (bp) oligonucleotide probes, it has been possible to identify nine different mutations in the DNA of 47 subjects from Turkey and Northern Cyprus with a beta-thalassemia homozygosity. The IVS-I nucleotide (nt) 110 G----A and the IVS-I nt 6 T----C substitutions and the frameshift at codon 8 were most frequently observed. Direct correlations were made between these data and clinical observations; mild disease was associated with homozygosity for IVS-I nt 6 T----C, for frameshift at codon 8, for the C----G substitution at nt -87, and for IVS-I nt 5 G----T, and for a double heterozygosity for some of these conditions. Moderate disease, observed in some of the patients, could be explained by combinations of specific mutations. All mutations were associated with specific haplotypes, while in some the observed beta zero-thalassemia was of the mild type due to a considerable production of Hb F.
通过基因扩增并与合成的19个碱基对(bp)寡核苷酸探针杂交的方法,已能够在来自土耳其和北塞浦路斯的47名β地中海贫血纯合子受试者的DNA中鉴定出9种不同的突变。IVS-I核苷酸(nt)110 G→A和IVS-I nt 6 T→C替换以及密码子8处的移码突变最为常见。这些数据与临床观察结果进行了直接关联;轻度疾病与IVS-I nt 6 T→C纯合子、密码子8处的移码突变、nt -87处的C→G替换、IVS-I nt 5 G→T以及其中一些情况的双重杂合子相关。在一些患者中观察到的中度疾病可以通过特定突变的组合来解释。所有突变都与特定的单倍型相关,而在一些情况下,观察到的β0地中海贫血由于Hb F的大量产生而属于轻度类型。