Kılıç Mustafa, Özgül Rıza Köksal, Dursun Ali, Tokatlı Ayşegül, Kalkanoğlu-Sivri Hatice Serap, Anlar Banu, Fowler Brian, Coşkun Turgay
Division of Hacettepe University Faculty of Medicine, Ankara, Turkey, and 3University Children's Hospital, Basel, Switzerland.
Turk J Pediatr. 2013 Nov-Dec;55(6):633-6.
Methylmalonic aciduria and homocystinuria, cobalamin C (cblC) type, is the most frequent inborn error of vitamin B12metabolism. The clinical phenotype includes systemic symptoms and neurological decompensation. Affected patients can be divided into two broad groups, as early-onset and late-onset. We present a Turkish patient who had neurological impairment at the age of four years as presented with late-onset cblC defect. Homozygous c.394C<T; p.R132* mutation in the MMACHC gene was detected. The patient was treated with hydroxocobalamin, betaine and folic acid combination with good clinical and biochemical response.
甲基丙二酸尿症和同型胱氨酸尿症,钴胺素C(cblC)型,是维生素B12代谢最常见的先天性缺陷。临床表型包括全身症状和神经功能失代偿。受影响的患者可分为两大类,即早发型和晚发型。我们报告一名土耳其患者,其在4岁时出现神经功能障碍,表现为晚发型cblC缺陷。检测到MMACHC基因纯合的c.394C<T;p.R132*突变。该患者接受了羟钴胺、甜菜碱和叶酸联合治疗,临床和生化反应良好。