Brown Elizabeth J, Pollak Martin R, Barua Moumita
Department of Pediatrics, University of Texas Southwestern Medical Center, Dallas, Texas, USA.
Department of Medicine, Beth Israel Deaconess Medical Center and Harvard Medical School, Boston, Massachusetts, USA.
Kidney Int. 2014 May;85(5):1030-8. doi: 10.1038/ki.2014.48. Epub 2014 Mar 5.
The haploid human genome is composed of three billion base pairs, about one percent of which consist of exonic regions, the coding sequence for functional proteins, also now known as the 'exome'. The development of next-generation sequencing makes it possible from a technical and economic standpoint to sequence an individual's exome but at the cost of generating long lists of gene variants that are not straightforward to interpret. Various public consortiums such as the 1000 Genomes Project and the NHLBI Exome Sequencing Project have sequenced the exomes and a subset of entire genomes of over 2500 control individuals with ongoing efforts to further catalog genetic variation in humans.(1) The use of these public databases facilitates the interpretation of these variant lists produced by exome sequencing and, as a result, novel genetic variants linked to the disease are being discovered and reported at a record rate. However, the interpretation of these results and their bearing on diagnosis, prognosis, and treatment is becoming even more complicated. Here, we discuss the application of genetic testing to individuals with focal and segmental glomerulosclerosis (FSGS), taking a historical perspective on gene identification and its clinical implications along with the growing potential of next-generation sequencing.
单倍体人类基因组由30亿个碱基对组成,其中约1% 由外显子区域构成,即功能性蛋白质的编码序列,如今也被称为 “外显子组”。新一代测序技术的发展,从技术和经济角度而言,使得对个体的外显子组进行测序成为可能,但代价是会生成一长串难以直接解读的基因变异列表。诸如千人基因组计划和美国国立心肺血液研究所外显子测序计划等多个公共联盟,已对2500多名对照个体的外显子组以及部分全基因组进行了测序,并且仍在持续努力进一步编目人类的基因变异情况。(1)这些公共数据库的使用有助于解读外显子测序产生的这些变异列表,因此,与疾病相关的新型基因变异正以前所未有的速度被发现和报道。然而,对这些结果的解读及其对诊断、预后和治疗的影响正变得愈发复杂。在此,我们从基因识别及其临床意义的历史视角以及新一代测序技术日益增长的潜力出发,探讨基因检测在局灶节段性肾小球硬化症(FSGS)患者中的应用。