Wong Sui-To, Ernest Kimberly, Fan Grace, Zovickian John, Pang Dachling
Department of Paediatric Neurosurgery, Regional Center for Paediatric Neurosurgery and.
J Neurosurg Pediatr. 2014 May;13(5):541-7. doi: 10.3171/2014.2.PEDS13527. Epub 2014 Mar 28.
Only 6 cases of isolated unilateral rupture of the alar ligament have been previously reported. The authors report a new case and review the literature, morbid anatomy, and pathogenesis of this rare injury. The patient in their case, a 9-year-old girl, fell head first from a height of 5 feet off the ground. She presented with neck pain, a leftward head tilt, and severe limitation of right rotation, extension, and right lateral flexion of the neck. Plain radiographs and CT revealed no fracture but a shift of the dens toward the right lateral mass of C-1. Magnetic resonance imaging of the cervical spine showed signal hyperintensity within the left dens-atlas space on both T1- and T2-weighted sequences and interruption of the expected dark signal representing the left alar ligament, suggestive of its rupture. After 12 weeks of immobilization in a Guilford brace, MRI showed lessened dens deviation, and the patient attained full and painless neck motion. Including the patient in this case, the 7 patients with this injury were between 5 and 21 years old, sustained the injury in traffic accidents or falls, presented with marked neck pain, and were treated with external immobilization. All patients had good clinical outcome. The mechanism of injury is hyperflexion with rotation. Isolated unilateral alar ligament rupture is a diagnosis made by excluding associated fracture, dislocation, or disruption of other major ligamentous structures in the craniovertebral junction. CT and MRI are essential in establishing the diagnosis. External immobilization is adequate treatment.
此前仅报道过6例孤立性单侧翼状韧带断裂的病例。作者报告了1例新病例,并对该罕见损伤的文献、病理解剖及发病机制进行了综述。他们病例中的患者是一名9岁女孩,从离地面5英尺的高度头部先着地摔倒。她表现为颈部疼痛、头部向左倾斜,以及颈部右旋转、伸展和右侧屈严重受限。X线平片和CT检查未发现骨折,但齿状突向C-1右侧块移位。颈椎磁共振成像显示,在T1加权和T2加权序列上,左侧齿突-寰椎间隙内信号增强,代表左翼状韧带的预期暗信号中断,提示其断裂。在使用吉尔福德支具固定12周后,MRI显示齿状突移位减轻,患者颈部活动完全恢复且无痛。包括该病例患者在内,7例该损伤患者年龄在5至21岁之间,均在交通事故或摔倒中受伤,表现为明显的颈部疼痛,接受了外固定治疗。所有患者临床结局良好。损伤机制为伴有旋转的过屈。孤立性单侧翼状韧带断裂是通过排除颅颈交界区相关骨折、脱位或其他主要韧带结构损伤而做出的诊断。CT和MRI对确诊至关重要。外固定是充分的治疗方法。