Sharma Pradeep Kumar, Saikia Bhaskar, Sharma Rachna, Ankur Kumar, Khilnani Praveen, Aggarwal Vinay Kumar, Cheong Hae
Department of Pediatric Intensive Care Unit, B L Kapur Super Speciality Hospital, New Delhi, India,
Indian J Pediatr. 2014 Oct;81(10):1095-8. doi: 10.1007/s12098-014-1379-6. Epub 2014 Apr 4.
Bartter syndrome is a group of inherited, salt-losing tubulopathies presenting as hypokalemic metabolic alkalosis with normotensive hyperreninemia and hyperaldosteronism. Around 150 cases have been reported in literature till now. Mutations leading to salt losing tubulopathies are not routinely tested in Indian population. The authors have done the genetic analysis for the first time in the Bartter syndrome on two cases from India. First case was antenatal Bartter syndrome presenting with massive polyuria and hyperkalemia. Mutational analysis revealed compound heterozygous mutations in KCNJ1(ROMK) gene [p(Leu220Phe), p(Thr191Pro)]. Second case had a phenotypic presentation of classical Bartter syndrome however, genetic analysis revealed only heterozygous novel mutation in SLC12A gene p(Ala232Thr). Bartter syndrome is a clinical diagnosis and genetic analysis is recommended for prognostication and genetic counseling.
巴特综合征是一组遗传性失盐性肾小管病,表现为低钾血症性代谢性碱中毒,伴有血压正常的高肾素血症和高醛固酮血症。迄今为止,文献报道了约150例病例。导致失盐性肾小管病的突变在印度人群中并非常规检测项目。作者首次对来自印度的两例巴特综合征患者进行了基因分析。第一例为产前巴特综合征,表现为大量多尿和高钾血症。突变分析显示KCNJ1(ROMK)基因存在复合杂合突变[p(Leu220Phe),p(Thr191Pro)]。第二例具有典型巴特综合征的表型表现,然而,基因分析仅发现SLC12A基因存在杂合新突变p(Ala232Thr)。巴特综合征是一种临床诊断,建议进行基因分析以用于预后评估和遗传咨询。