Kato Takema, Franconi Colleen P, Sheridan Molly B, Hacker April M, Inagakai Hidehito, Glover Thomas W, Arlt Martin F, Drabkin Harry A, Gemmill Robert M, Kurahashi Hiroki, Emanuel Beverly S
Division of Human Genetics, The Children's Hospital of Philadelphia, Philadelphia, PA, USA.
Division of Molecular Genetics, Institute for Comprehensive Medical Science, Fujita Health University, Aichi, Japan.
Cancer Genet. 2014 Apr;207(4):133-40. doi: 10.1016/j.cancergen.2014.03.004. Epub 2014 Mar 18.
It has emerged that palindrome-mediated genomic instability generates DNA-based rearrangements. The presence of palindromic AT-rich repeats (PATRRs) at the translocation breakpoints suggested a palindrome-mediated mechanism in the generation of several recurrent constitutional rearrangements: the t(11;22), t(17;22), and t(8;22). To date, all reported PATRR-mediated translocations include the PATRR on chromosome 22 (PATRR22) as a translocation partner. Here, the constitutional rearrangement, t(3;8)(p14.2;q24.1), segregating with renal cell carcinoma in two families, is examined. The chromosome 8 breakpoint lies in PATRR8 in the first intron of the RNF139 (TRC8) gene, whereas the chromosome 3 breakpoint is located in an AT-rich palindromic sequence in intron 3 of the FHIT gene (PATRR3). Thus, the t(3;8) is the first PATRR-mediated, recurrent, constitutional translocation that does not involve PATRR22. Furthermore, we detect de novo translocations similar to the t(11;22) and t(8;22), involving PATRR3 in normal sperm. The breakpoint on chromosome 3 is in proximity to FRA3B, the most common fragile site in the human genome and a site of frequent deletions in tumor cells. However, the lack of involvement of PATRR3 sequence in numerous FRA3B-related deletions suggests that there are several different DNA sequence-based etiologies responsible for chromosome 3p14.2 genomic rearrangements.
已发现回文介导的基因组不稳定性会产生基于DNA的重排。在易位断点处存在富含AT的回文重复序列(PATRRs),这表明在几种复发性染色体结构重排(t(11;22)、t(17;22)和t(8;22))的产生过程中存在回文介导的机制。迄今为止,所有报道的PATRR介导的易位都包括22号染色体上的PATRR(PATRR22)作为易位伙伴。在此,对在两个家族中与肾细胞癌分离的染色体结构重排t(3;8)(p14.2;q24.1)进行了研究。8号染色体断点位于RNF139(TRC8)基因第一内含子中的PATRR8内,而3号染色体断点位于FHIT基因第3内含子中的富含AT的回文序列(PATRR3)中。因此,t(3;8)是第一个不涉及PATRR22的PATRR介导的、复发性的染色体结构易位。此外,我们在正常精子中检测到了类似于t(11;22)和t(8;22)的新生易位,涉及PATRR3。3号染色体上的断点靠近FRA3B,FRA3B是人类基因组中最常见的脆性位点,也是肿瘤细胞中频繁缺失的位点。然而,在许多与FRA3B相关的缺失中未涉及PATRR3序列,这表明有几种不同的基于DNA序列的病因导致3p14.2染色体基因组重排。