Turki I, Kresse H, Scotto J, Tardieu M
Département de Pédiatrie, Hôpital de Bicêtre, Le Kremlin-Bicêtre, France.
Neuropediatrics. 1989 May;20(2):90-2. doi: 10.1055/s-2008-1071272.
Six siblings were followed, three of them suffering from a Sanfilippo disease, type C, as demonstrated by a deficient glucosamine acetyltransferase activity in cultured skin fibroblasts. Clinical and radiological findings were similar in the three affected children and the phenotypical expression of the disease allowed no distinction between the different types of Sanfilippo disease. Ultrastructural studies of the liver demonstrated characteristic intra-vacuolar inclusions.
对六名兄弟姐妹进行了跟踪观察,其中三人患有C型Sanfilippo病,培养的皮肤成纤维细胞中氨基葡萄糖乙酰转移酶活性不足证明了这一点。三名患病儿童的临床和放射学表现相似,该疾病的表型表达无法区分不同类型的Sanfilippo病。肝脏的超微结构研究显示出特征性的空泡内包涵体。