Schulze Franziska S, Beckmann Tina, Nimmerjahn Falk, Ishiko Akira, Collin Mattias, Köhl Jörg, Goletz Stephanie, Zillikens Detlef, Ludwig Ralf, Schmidt Enno
Department of Dermatology, University of Lübeck, Lübeck, Germany.
Department of Biology, University of Erlangen-Nuremberg, Erlangen, Germany.
Am J Pathol. 2014 Aug;184(8):2185-96. doi: 10.1016/j.ajpath.2014.05.007.
Bullous pemphigoid (BP) and epidermolysis bullosa acquisita are subepidermal autoimmune blistering diseases mediated by autoantibodies against type XVII collagen (Col17) and Col7, respectively. For blister formation, Fc-mediated events, such as infiltration of inflammatory cells in the skin, complement activation, and release of proteases at the dermal-epidermal junction, are essential. Although in the neonatal passive transfer mouse model of BP, tissue destruction is mediated by Fcγ receptors (FcγRs) I and III, the passive transfer model of epidermolysis bullosa acquisita completely depends on FcγRIV. To clarify this discrepancy, we developed a novel experimental model for BP using adult mice. Lesion formation was Fc mediated because γ-chain-deficient mice and mice treated with anti-Col17 IgG, depleted from its sugar moiety at the Fc portion, were resistant to disease induction. By the use of various FcγR-deficient mouse strains, tissue destruction was shown to be mediated by FcγRIV, FcγRIII, and FcγRIIB, whereas FcγRI was not essential. Furthermore, anti-inflammatory mediators in already clinically diseased mice can be explored in the novel BP model, because the pharmacological inhibition of FcγRIV and depletion of granulocytes abolished skin blisters. Herein, we extended our knowledge about the importance of FcγRs in experimental BP and established a novel BP mouse model suitable to study disease development over a longer time period and explore novel treatment strategies in a quasi-therapeutic setting.
大疱性类天疱疮(BP)和获得性大疱性表皮松解症是分别由针对 XVII 型胶原蛋白(Col17)和 VII 型胶原蛋白(Col7)的自身抗体介导的表皮下自身免疫性水疱病。对于水疱形成,Fc 介导的事件,如皮肤中炎性细胞的浸润、补体激活以及在真皮-表皮交界处蛋白酶的释放,是必不可少的。尽管在 BP 的新生儿被动转移小鼠模型中,组织破坏是由 Fcγ 受体(FcγRs)I 和 III 介导的,但获得性大疱性表皮松解症的被动转移模型完全依赖于 FcγRIV。为了阐明这种差异,我们使用成年小鼠开发了一种新型的 BP 实验模型。病变形成是由 Fc 介导的,因为 γ 链缺陷小鼠和用从 Fc 部分去除糖基的抗 Col17 IgG 处理的小鼠对疾病诱导具有抗性。通过使用各种 FcγR 缺陷小鼠品系,发现组织破坏是由 FcγRIV、FcγRIII 和 FcγRIIB 介导的,而 FcγRI 并非必需。此外,在已经患有临床疾病的小鼠中可以探索抗炎介质,因为对 FcγRIV 的药理抑制和粒细胞的清除消除了皮肤水疱。在此,我们扩展了关于 FcγRs 在实验性 BP 中的重要性的认识,并建立了一种新型的 BP 小鼠模型,适用于在更长时间内研究疾病发展并在准治疗环境中探索新的治疗策略。