Baretić Maja, Korsić Mirko, Potocki Kristina, Horvatić Gordana Herceg, Orlić Zeljka Crncević
Coll Antropol. 2014 Jun;38(2):755-8.
34-year old patient had history of muscular wasting, easy fatigability, pain in extremities and waddling gait since age of four. During the time, neuromuscular disease was suspected, but not confirmed. Elevated bone alkaline phosphatase as well as other bone turnover markers (osteocalcin, procollagen, telopeptide) indicated further skeletal evaluation. Symmetrical enhanced uptake on technetium methylene diphosphonate [99mTc]MPD bone scintigraphy at diaphyses of longitudinal bones and scull matched cortical thickening of long bones and sclerosis of the scull seen at radiograms. Those findings pointed to Camurati-Engelmann disease misdiagnosed for the long time. This rare genetic autosomal dominant disorder was retrospectively diagnosed in asymptomatic father too on the basis of bone scans done long time ago. Old family member scans confirmed heredity pattern of the disease.
一名34岁患者自4岁起就有肌肉萎缩、易疲劳、四肢疼痛和蹒跚步态的病史。在此期间,怀疑患有神经肌肉疾病,但未得到确诊。骨碱性磷酸酶以及其他骨转换标志物(骨钙素、前胶原、端肽)升高,提示需要进一步进行骨骼评估。锝亚甲基二膦酸盐[99mTc]MPD骨闪烁显像显示,长骨骨干和颅骨的对称性摄取增强,这与X线片上所见的长骨皮质增厚和颅骨硬化相匹配。这些发现表明,长期以来被误诊为卡-恩病。根据很久以前进行的骨扫描,在无症状的父亲身上也回顾性诊断出了这种罕见的常染色体显性遗传病。对家族中长辈的扫描证实了该病的遗传模式。