Li Lin, Li Xiao, Liu Yongchao, Zheng Shuqi, Zhang Jixia, Liu Qiji, Heng Xueyuan
Institute of Genetics, Linyi People's Hospital, Linyi, Shandong 276000, P. R. China.
Zhonghua Yi Xue Yi Chuan Xue Za Zhi. 2014 Dec;31(6):743-6. doi: 10.3760/cma.j.issn.1003-9406.2014.06.013.
To investigate EXT1 and EXT2 genes mutations in a family with hereditary multiple osteochondromas (HME).
A four-generation family with HME from Linyi city of Shandong Province was studied. There were 6 affected individuals among the 17 family members. Physical examination and radiographical evaluations were carried out for all family members. Genomic DNA was extracted from peripheral venous blood and the samples were subjected to mutation screening by PCR of the coding regions of EXT1 and EXT2 genes.
The family has featured an autosomal dominant inheritance pattern. Sequencing of the EXT1 and EXT2 genes suggested the causative gene in this family was in linkage with the second exon of EXT2. A c.244delG mutation was detected, which has resulted in a frameshift mutation p.Asp81IlefsX30. The mutation was found in all of the 6 affected individuals but not in normal family members. And the mutation has co-segregated with the phenotype.
The mutation c.244delG in the EXT2 gene is the probably the cause of the disease in this family.
研究一个遗传性多发性骨软骨瘤(HME)家系中EXT1和EXT2基因的突变情况。
对来自山东省临沂市的一个四代HME家系进行研究。该家系17名成员中有6名患病个体。对所有家庭成员进行了体格检查和影像学评估。从外周静脉血中提取基因组DNA,并通过PCR对EXT1和EXT2基因的编码区进行突变筛查。
该家系呈现常染色体显性遗传模式。EXT1和EXT2基因测序表明,该家系的致病基因与EXT2基因的第二个外显子连锁。检测到一个c.244delG突变,该突变导致了移码突变p.Asp81IlefsX30。该突变在所有6名患病个体中均被发现,而在正常家庭成员中未发现。并且该突变与表型共分离。
EXT2基因中的c.244delG突变可能是该家系疾病的病因。