Song Yanmin, Liu Yunhai, Zhang Ning, Long Lili
Department of Neurology, Xiangya Hospital, Central South University, Changsha, Hunan 410008, P.R. China.
Exp Ther Med. 2015 Feb;9(2):417-420. doi: 10.3892/etm.2014.2136. Epub 2014 Dec 16.
The aim of the present study was to conduct a familial investigation and provide a genetic diagnosis to a family presenting with spastic paraplegia and clinically diagnosed with hereditary spastic paraplegia (HSP). Blood samples were obtained from the family, and mutations in the gene causing spinocerebellar ataxia type 3 (SCA3)/Machado-Joseph disease (MJD), known as MJD1, were analyzed using the polymerase chain reaction, 8% denaturing polyacrylamide gel electrophoresis, and T-vector ligation and sequencing. The trinucleotide repeat number of the mutant allele was 80, leading to a genetic diagnosis of SCA3/MJD. This suggests that patients with SCA3/MJD characteristically present with typical spastic paraplegia without evident manifestations of ataxia. For those families with HSP involving the nervous system and showing genetic anticipation, an MJD1 genetic diagnosis should be considered to assist in clinical diagnosis of HSP.
本研究的目的是对一个表现为痉挛性截瘫且临床诊断为遗传性痉挛性截瘫(HSP)的家庭进行家系调查并提供基因诊断。从该家庭采集血样,使用聚合酶链反应、8%变性聚丙烯酰胺凝胶电泳、T载体连接和测序分析导致3型脊髓小脑共济失调(SCA3)/马查多-约瑟夫病(MJD)(即MJD1基因)的突变。突变等位基因的三核苷酸重复数为80,从而得出SCA3/MJD的基因诊断。这表明SCA3/MJD患者典型地表现为典型的痉挛性截瘫,无明显共济失调表现。对于那些患有累及神经系统且显示遗传早现的HSP家庭,应考虑进行MJD1基因诊断以协助HSP的临床诊断。