Suppr超能文献

对乳腺癌家系登记处临床确诊家系中的PALB2进行突变筛查。

Mutation screening of PALB2 in clinically ascertained families from the Breast Cancer Family Registry.

作者信息

Nguyen-Dumont Tú, Hammet Fleur, Mahmoodi Maryam, Tsimiklis Helen, Teo Zhi L, Li Roger, Pope Bernard J, Terry Mary Beth, Buys Saundra S, Daly Mary, Hopper John L, Winship Ingrid, Goldgar David E, Park Daniel J, Southey Melissa C

机构信息

Genetic Epidemiology Laboratory, Department of Pathology, The University of Melbourne, Melbourne, VIC, 3010, Australia,

出版信息

Breast Cancer Res Treat. 2015 Jan;149(2):547-54. doi: 10.1007/s10549-014-3260-8. Epub 2015 Jan 10.

Abstract

Loss-of-function mutations in PALB2 are associated with an increased risk of breast cancer, with recent data showing that female breast cancer risks for PALB2 mutation carriers are comparable in magnitude to those for BRCA2 mutation carriers. This study applied targeted massively parallel sequencing to characterize the mutation spectrum of PALB2 in probands attending breast cancer genetics clinics in the USA. The coding regions and proximal intron-exon junctions of PALB2 were screened in probands not known to carry a mutation in BRCA1 or BCRA2 from 1,250 families enrolled through familial cancer clinics by the Breast Cancer Family Registry. Mutation screening was performed using Hi-Plex, an amplicon-based targeted massively parallel sequencing platform. Screening of PALB2 was successful in 1,240/1,250 probands and identified nine women with protein-truncating mutations (three nonsense mutations and five frameshift mutations). Four of the 33 missense variants were predicted to be deleterious to protein function by in silico analysis using two different programs. Analysis of tumors from carriers of truncating mutations revealed that the majority were high histological grade, invasive ductal carcinomas. Young onset was apparent in most families, with 19 breast cancers under 50 years of age, including eight under the age of 40 years. Our data demonstrate the utility of Hi-Plex in the context of high-throughput testing for rare genetic mutations and provide additional timely information about the nature and prevalence of PALB2 mutations, to enhance risk assessment and risk management of women at high risk of cancer attending clinical genetic services.

摘要

PALB2功能缺失突变与乳腺癌风险增加相关,近期数据表明,PALB2突变携带者患女性乳腺癌的风险在程度上与BRCA2突变携带者相当。本研究应用靶向大规模平行测序技术,对美国乳腺癌遗传学诊所的先证者中PALB2的突变谱进行了特征分析。通过乳腺癌家族登记处从1250个家庭的家族癌症诊所招募的先证者中,对已知未携带BRCA1或BCRA2突变的个体进行PALB2编码区及近端内含子-外显子连接区的筛查。使用Hi-Plex(一种基于扩增子的靶向大规模平行测序平台)进行突变筛查。在1250名先证者中的1240名中成功完成了PALB2筛查,鉴定出9名携带蛋白质截短突变的女性(3个无义突变和5个移码突变)。使用两个不同程序进行的计算机分析预测,33个错义变体中的4个对蛋白质功能有害。对截短突变携带者的肿瘤分析显示,大多数为高组织学分级的浸润性导管癌。大多数家族中发病年龄较轻,有19例乳腺癌患者年龄在50岁以下,其中8例年龄在40岁以下。我们的数据证明了Hi-Plex在罕见基因突变高通量检测中的实用性,并提供了关于PALB2突变性质和患病率的更多及时信息,以加强对临床遗传服务中癌症高危女性的风险评估和风险管理。

相似文献

4
Mutation analysis of PALB2 gene in French breast cancer families.法国乳腺癌家族中PALB2基因的突变分析
Breast Cancer Res Treat. 2015 Dec;154(3):463-71. doi: 10.1007/s10549-015-3625-7. Epub 2015 Nov 12.
6
PALB2 analysis in BRCA2-like families.PALB2 分析在 BRCA2 样家族中。
Breast Cancer Res Treat. 2011 Jun;127(2):357-62. doi: 10.1007/s10549-010-1001-1. Epub 2010 Jun 26.

引用本文的文献

本文引用的文献

6
PALB2 and breast cancer: ready for clinical translation!PALB2与乳腺癌:准备好进行临床转化了!
Appl Clin Genet. 2013 Jul 19;6:43-52. doi: 10.2147/TACG.S34116. Print 2013.
8
Tumour morphology predicts PALB2 germline mutation status.肿瘤形态可预测 PALB2 种系突变状态。
Br J Cancer. 2013 Jul 9;109(1):154-63. doi: 10.1038/bjc.2013.295. Epub 2013 Jun 20.
10

文献AI研究员

20分钟写一篇综述,助力文献阅读效率提升50倍。

立即体验

用中文搜PubMed

大模型驱动的PubMed中文搜索引擎

马上搜索

文档翻译

学术文献翻译模型,支持多种主流文档格式。

立即体验