Hakim Kaouthar, Boussaada Rafik, Ayari Jihen, Imen Hamdi, Msaad Hela, Ouarda Fatma, Chaker Lilia
Cardiol Tunis. 2013 Oct;9(4):73-76.
Ebstein's disease with functional pulmonary atresia is a severe neonatal presentation of Ebstein's anomaly where the therapeutic management is typically based on the prescription of prostaglandins. The circular shunt is a serious "hemodynamic" complication which is often undiagnosed leading to the discontinuation of prostaglandins. We report a severe neonatal form of Ebstein's anomaly with hemodynamic deterioration relatted to a circular shunt. The diagnosis of Ebstein's anomaly with functional pulmonary atresia was made prenatally at 36 weeks of pregnancy. The patient was born at 38 weeks of gestation by caesarean section. Postnatal ultrasound confirmed the diagnosis. Treatment with prostaglandins was originally created to maintain the vital ductus arteriosus patent. Despite this treatment, hemodynamic deterioration was observed. Ultrasound monitoring showed pictures for a circular shunt. Indeed, blood coming into the pulmonary artery by the wide ductus arteriosus, was "drawn" to the right ventricle and the right atrium due to tricuspid regurgitation and from there to the left heart via the fossa ovalis shunting right to left, when it was ejected into the aorta and the ductus arteriosus. Before this circular shunt, treatment with prostaglandin was discontinued and treatment to reduce pulmonary resistance was described. However, the patient died prior to initiation of treatment. The neonatal form of Ebstein's anomaly is a severe form that can be complicated by a circular shunt. This hemodynamic phenomenon encourages early closure of the ductus arteriosus against indicating the prescription of prostaglandins.
埃布斯坦畸形合并功能性肺动脉闭锁是埃布斯坦畸形的一种严重新生儿表现形式,其治疗管理通常基于前列腺素的处方。环状分流是一种严重的“血流动力学”并发症,常常未被诊断出来,导致前列腺素停用。我们报告了一例严重的新生儿埃布斯坦畸形,其血流动力学恶化与环状分流有关。埃布斯坦畸形合并功能性肺动脉闭锁在妊娠36周时产前确诊。患者在妊娠38周时通过剖宫产出生。产后超声证实了诊断。最初使用前列腺素治疗是为了维持动脉导管开放。尽管进行了这种治疗,但仍观察到血流动力学恶化。超声监测显示存在环状分流的图像。实际上,通过宽大的动脉导管进入肺动脉的血液,由于三尖瓣反流,被“吸引”到右心室和右心房,然后通过卵圆孔从右向左分流到左心,再被射入主动脉和动脉导管。在出现这种环状分流之前,停用了前列腺素治疗,并描述了降低肺阻力的治疗方法。然而,患者在开始治疗前死亡。新生儿埃布斯坦畸形是一种严重形式,可并发环状分流。这种血流动力学现象促使动脉导管早期关闭,反对使用前列腺素处方。