Berggren Kiersten L, Chen Jianfang, Fox Julia, Miller Jonathan, Dodds Lindsay, Dugas Bryan, Vargas Liset, Lothian Amber, McAllum Erin, Volitakis Irene, Roberts Blaine, Bush Ashley I, Fox Jonathan H
Department of Veterinary Sciences, University of Wyoming, 1174 Snowy Range Road, Laramie, WY 82070, USA.
Department of Veterinary Sciences, University of Wyoming, 1174 Snowy Range Road, Laramie, WY 82070, USA; Neuroscience Graduate Program, University of Wyoming, 1174 Snowy Range Road, Laramie, WY 82070, USA.
Redox Biol. 2015;4:363-74. doi: 10.1016/j.redox.2015.02.002. Epub 2015 Feb 11.
Huntington's disease (HD) is a progressive neurodegenerative disorder caused by a CAG repeat expansion that encodes a polyglutamine tract in huntingtin (htt) protein. Dysregulation of brain iron homeostasis, oxidative stress and neurodegeneration are consistent features of the HD phenotype. Therefore, environmental factors that exacerbate oxidative stress and iron dysregulation may potentiate HD. Iron supplementation in the human population is common during infant and adult-life stages. In this study, iron supplementation in neonatal HD mice resulted in deterioration of spontaneous motor running activity, elevated levels of brain lactate and oxidized glutathione consistent with increased energetic dysfunction and oxidative stress, and increased striatal and motor cortical neuronal atrophy, collectively demonstrating potentiation of the disease phenotype. Oxidative stress, energetic, and anatomic markers of degeneration were not affected in wild-type littermate iron-supplemented mice. Further, there was no effect of elevated iron intake on disease outcomes in adult HD mice. We have demonstrated an interaction between the mutant huntingtin gene and iron supplementation in neonatal HD mice. Findings indicate that elevated neonatal iron intake potentiates mouse HD and promotes oxidative stress and energetic dysfunction in brain. Neonatal-infant dietary iron intake level may be an environmental modifier of human HD.
亨廷顿舞蹈症(HD)是一种由CAG重复序列扩增引起的进行性神经退行性疾病,该扩增序列编码亨廷顿蛋白(htt)中的一段多聚谷氨酰胺序列。脑铁稳态失调、氧化应激和神经退行性变是HD表型的一致特征。因此,加剧氧化应激和铁失调的环境因素可能会加重HD。在人类婴儿期和成年期,补充铁剂很常见。在本研究中,给新生HD小鼠补充铁剂导致自发运动活动恶化、脑乳酸水平升高以及氧化型谷胱甘肽增加,这与能量功能障碍和氧化应激增加一致,同时纹状体和运动皮层神经元萎缩增加,共同表明疾病表型增强。在补充铁剂的野生型同窝小鼠中,氧化应激、能量和变性的解剖学标志物未受影响。此外,成年HD小鼠铁摄入量增加对疾病结局没有影响。我们已经证明了新生HD小鼠中突变的亨廷顿基因与补充铁剂之间的相互作用。研究结果表明,新生儿期铁摄入量增加会增强小鼠HD,并促进大脑中的氧化应激和能量功能障碍。新生儿-婴儿期的膳食铁摄入量可能是人类HD的一个环境调节因素。