Okuno Takashi, Tokuriki Shuko, Yoshino Tomomi, Tanaka Nanae, Ohshima Yusei
Department of Pediatrics, Faculty of Medical Sciences, University of Fukui, Fukui, Japan.
Pediatr Int. 2015 Apr;57(2):e34-6. doi: 10.1111/ped.12517.
Diffuse neonatal hemangiomatosis (DNH) is a rare condition characterized by the concomitant development of multiple cutaneous infantile hemangiomas (IH) and visceral hemangiomas. Recently, an association between erythropoietin treatment and an increased incidence of infantile hemangioma was noted. A Japanese male infant was born via cesarean section at 27 weeks of gestation. Following the commencement of erythropoietin treatment for anemia of prematurity, he developed multiple cutaneous hemangiomas, high cardiac output heart failure and hepatomegaly. Abdominal imaging indicated comorbidity of diffuse infantile hepatic hemannigomas, resulting in the final diagnosis of DNH. The discontinuation of erythropoietin treatment and long-term therapy with propranolol improved the hepatic lesions and cutaneous hemangiomas. The possibility of multiple organ involvement and the exacerbating effects of erythropoietin treatment should be considered in cases in which multiple cutaneous hemangiomas develop in preterm infants receiving erythropoietin treatment.
弥漫性新生儿血管瘤病(DNH)是一种罕见疾病,其特征为多发性皮肤婴儿血管瘤(IH)和内脏血管瘤同时发生。最近,有人注意到促红细胞生成素治疗与婴儿血管瘤发病率增加之间存在关联。一名日本男婴在妊娠27周时通过剖宫产出生。在开始使用促红细胞生成素治疗早产儿贫血后,他出现了多发性皮肤血管瘤、高心输出量心力衰竭和肝肿大。腹部影像学检查显示存在弥漫性婴儿肝血管瘤合并症,最终诊断为DNH。停用促红细胞生成素治疗并使用普萘洛尔进行长期治疗后,肝脏病变和皮肤血管瘤有所改善。对于接受促红细胞生成素治疗的早产儿出现多发性皮肤血管瘤的情况,应考虑多器官受累的可能性以及促红细胞生成素治疗的加重作用。