Tarasenko Tatyana N, Singh Larry N, Chatterji-Len Milani, Zerfas Patricia M, Cusmano-Ozog Kristina, McGuire Peter J
Metabolism, Infection and Immunity Unit, National Human Genome Research Institute, National Institutes of Health, Bethesda, MD, USA.
Center for Mitochondrial and Epigenomic Medicine, Department of Pathology, Children's Hospital of Philadelphia, Philadelphia, PA, USA.
Biochim Biophys Acta. 2015 Nov;1852(11):2391-401. doi: 10.1016/j.bbadis.2015.08.021. Epub 2015 Aug 28.
In response to infection, patients with inborn errors of metabolism may develop a functional deterioration termed metabolic decompensation. The biochemical hallmarks of this disruption of metabolic homeostasis are disease specific and may include acidosis, hyperammonemia or hypoglycemia. In a model system previously published by our group, we noted that during influenza infection, mice displayed a depression in hepatic mitochondrial enzymes involved in nitrogen metabolism. Based on these findings, we hypothesized that this normal adaptation may extend to other metabolic pathways, and as such, may impact various inborn errors of metabolism. Since the liver is a critical organ in inborn errors of metabolism, we carried out untargeted metabolomic profiling of livers using mass spectrometry in C57Bl/6 mice infected with influenza to characterize metabolic adaptation. Pathway analysis of metabolomic data revealed reductions in CoA synthesis, and long chain fatty acyl CoA and carnitine species. These metabolic adaptations coincided with a depression in hepatic long chain β-oxidation mRNA and protein. To our surprise, the metabolic changes observed occurred in conjunction with a hepatic innate immune response, as demonstrated by transcriptional profiling and flow cytometry. By employing an immunomodulation strategy to deplete Kupffer cells, we were able to improve the expression of multiple genes involved in β-oxidation. Based on these findings, we are the first to suggest that the role of the liver as an immunologic organ is central in the pathophysiology of hepatic metabolic decompensation in inborn errors of metabolism due to respiratory viral infection.
针对感染,患有先天性代谢缺陷的患者可能会出现一种称为代谢失代偿的功能恶化。这种代谢稳态破坏的生化特征具有疾病特异性,可能包括酸中毒、高氨血症或低血糖。在我们小组之前发表的一个模型系统中,我们注意到在流感感染期间,小鼠肝脏中参与氮代谢的线粒体酶表现出活性降低。基于这些发现,我们推测这种正常的适应性反应可能会扩展到其他代谢途径,因此可能会影响各种先天性代谢缺陷。由于肝脏是先天性代谢缺陷中的关键器官,我们对感染流感的C57Bl/6小鼠肝脏进行了非靶向代谢组学分析,以质谱法表征代谢适应性。代谢组学数据的通路分析显示辅酶A合成、长链脂肪酰辅酶A和肉碱种类减少。这些代谢适应性变化与肝脏长链β-氧化的mRNA和蛋白质表达降低相一致。令我们惊讶的是,观察到的代谢变化与肝脏先天性免疫反应同时发生,转录谱分析和流式细胞术证明了这一点。通过采用免疫调节策略清除库普弗细胞,我们能够改善参与β-氧化的多个基因的表达。基于这些发现,我们首次提出,在因呼吸道病毒感染导致的先天性代谢缺陷中,肝脏作为免疫器官的作用在肝脏代谢失代偿的病理生理学中至关重要。