Ali Robert, Baldeo Candice, Onyenekwe Jesse, Lala Roshan, Landa Cristian, Siddiqi Anwer
Department of Internal Medicine, University of Florida, Jacksonville, USA.
Department of Pathology, University of Florida, Jacksonville, USA.
Case Rep Rheumatol. 2015;2015:513602. doi: 10.1155/2015/513602. Epub 2015 Aug 11.
Granulomatosis with polyangiitis (GPA), previously termed Wegener's Granulomatosis, is an autoimmune small vessel vasculitis which is highly associated with antineutrophil cytoplasmic antibodies (ANCA) and has varied clinical manifestations. Diagnosis hinges on identifying a combination of clinical features of systemic vasculitis, positive ANCA serology, and histological evidence of necrotizing vasculitis, necrotizing glomerulonephritis, or granulomatous inflammation from a relevant organ biopsy. The American College of Rheumatology has also developed a classification criteria focusing specifically on nasal or oral inflammation, abnormal chest radiograph, and abnormal urinary sediment, along with granulomatous inflammation, which helps to distinguish GPA from other forms of systemic vasculitis. In the case presented below, the diagnosis of GPA was delayed as the patient had a concomitant atypical endobronchial carcinoid which predisposed to postobstructive pneumonia. Fortunately, the papular lesions that developed across her lower limbs prompted further investigations. The return of appropriate serology coincided with progression to alveolar hemorrhage, offering a more complete clinical picture, and when she responded to the combination of steroid, cyclophosphamide, and plasma exchange, the diagnosis of GPA was cinched.
肉芽肿性多血管炎(GPA),以前称为韦格纳肉芽肿,是一种自身免疫性小血管炎,与抗中性粒细胞胞浆抗体(ANCA)高度相关,临床表现多样。诊断取决于识别系统性血管炎的临床特征组合、ANCA血清学阳性以及相关器官活检显示的坏死性血管炎、坏死性肾小球肾炎或肉芽肿性炎症的组织学证据。美国风湿病学会还制定了专门针对鼻或口腔炎症、胸部X线异常、尿沉渣异常以及肉芽肿性炎症的分类标准,这有助于将GPA与其他形式的系统性血管炎区分开来。在下面介绍的病例中,GPA的诊断被延迟,因为患者同时患有非典型支气管内类癌,易引发阻塞性肺炎。幸运的是,患者下肢出现的丘疹性病变促使进一步检查。合适的血清学结果出现之时恰逢病情进展为肺泡出血,从而呈现出更完整的临床情况,并且当她对类固醇、环磷酰胺和血浆置换的联合治疗产生反应时,GPA的诊断得以确定。