Wilcox David A
Department of Pediatrics, Medical College of Wisconsin, Milwaukee, WI; Children's Research Institute, Children's Hospital of Wisconsin, Milwaukee, WI; and Blood Research Institute, BloodCenter of Wisconsin, Milwaukee, WI.
Blood. 2016 Mar 10;127(10):1260-8. doi: 10.1182/blood-2015-07-607937. Epub 2016 Jan 19.
Hematopoietic stem cells (HSCs) can be safely collected from the body, genetically modified, and re-infused into a patient with the goal to express the transgene product for an individual's lifetime. Hematologic defects that can be corrected with an allogeneic bone marrow transplant can theoretically also be treated with gene replacement therapy. Because some genetic disorders affect distinct cell lineages, researchers are utilizing HSC gene transfer techniques using lineage-specific endogenous gene promoters to confine transgene expression to individual cell types (eg, ITGA2B for inherited platelet defects). HSCs appear to be an ideal target for platelet gene therapy because they can differentiate into megakaryocytes which are capable of forming several thousand anucleate platelets that circulate within blood vessels to establish hemostasis by repairing vascular injury. Platelets play an essential role in other biological processes (immune response, angiogenesis) as well as diseased states (atherosclerosis, cancer, thrombosis). Thus, recent advances in genetic manipulation of megakaryocytes could lead to new and improved therapies for treating a variety of disorders. In summary, genetic manipulation of megakaryocytes has progressed to the point where clinically relevant strategies are being developed for human trials for genetic disorders affecting platelets. Nevertheless, challenges still need to be overcome to perfect this field; therefore, strategies to increase the safety and benefit of megakaryocyte gene therapy will be discussed.
造血干细胞(HSCs)可以从体内安全采集,进行基因改造,然后重新注入患者体内,目的是使转基因产物在个体的一生中持续表达。理论上,能用异基因骨髓移植纠正的血液学缺陷也可以通过基因替代疗法来治疗。由于一些遗传疾病会影响不同的细胞谱系,研究人员正在利用造血干细胞基因转移技术,使用谱系特异性内源性基因启动子将转基因表达限制在个别细胞类型中(例如,用于遗传性血小板缺陷的整合素α2β(ITGA2B))。造血干细胞似乎是血小板基因治疗的理想靶点,因为它们可以分化为巨核细胞,巨核细胞能够形成数千个无核血小板,这些血小板在血管内循环,通过修复血管损伤来实现止血。血小板在其他生物学过程(免疫反应、血管生成)以及疾病状态(动脉粥样硬化、癌症、血栓形成)中也发挥着重要作用。因此,巨核细胞基因操作的最新进展可能会带来用于治疗多种疾病的新的、改进的疗法。总之,巨核细胞的基因操作已经发展到正在为影响血小板的遗传疾病开发用于人体试验的临床相关策略的阶段。然而,要完善这个领域仍需克服挑战;因此,将讨论提高巨核细胞基因治疗安全性和效益的策略。